Literature DB >> 32067119

Carnitine Palmitoyl Transferase Deficiency in a University Immunology Practice.

Kiley Bax1, Paul J Isackson2, Molly Moore3, Julian L Ambrus4,5.   

Abstract

PURPOSE: This report describes the clinical manifestations of 35 patients sent to a University Immunology clinic with a diagnosis of fatigue and exercise intolerance who were identified to have low carnitine palmitoyl transferase activity on muscle biopsies. RECENT
FINDINGS: All of the patients presented with fatigue and exercise intolerance and many had been diagnosed with fibromyalgia. Their symptoms responded to treatment of the metabolic disease. Associated symptoms included bloating, diarrhea, constipation, gastrointestinal reflux symptoms, recurrent infections, arthritis, dyspnea, dry eye, visual loss, and hearing loss. Associated medical conditions included Hashimoto thyroiditis, Sjogren's syndrome, seronegative arthritis, food hypersensitivities, asthma, sleep apnea, and vasculitis. This study identifies clinical features that should alert physicians to the possibility of an underlying metabolic disease. Treatment of the metabolic disease leads to symptomatic improvement.

Entities:  

Keywords:  Asthma; Carnitine palmitoyl transferase; Gastrointestinal dysmotility; Mitochondria; Raynaud’s; Sjogren’s syndrome

Mesh:

Substances:

Year:  2020        PMID: 32067119     DOI: 10.1007/s11926-020-0879-9

Source DB:  PubMed          Journal:  Curr Rheumatol Rep        ISSN: 1523-3774            Impact factor:   4.592


  97 in total

Review 1.  Carnitine palmitoyltransferase II deficiency with a focus on newborn screening.

Authors:  Go Tajima; Keiichi Hara; Miori Yuasa
Journal:  J Hum Genet       Date:  2018-12-04       Impact factor: 3.172

Review 2.  Sjogren's syndrome.

Authors:  Fotini C Soliotis; Haralampos M Moutsopoulos
Journal:  Autoimmunity       Date:  2004-06       Impact factor: 2.815

3.  Gastrointestinal complications of mitochondrial disease.

Authors:  Xenia B Hom; Joel E Lavine
Journal:  Mitochondrion       Date:  2004-09       Impact factor: 4.160

4.  Novel insights into systemic autoimmune rheumatic diseases using shared molecular signatures and an integrative analysis.

Authors:  Marie Hudson; Sasha Bernatsky; Ines Colmegna; Maximilien Lora; Tomi Pastinen; Kathleen Klein Oros; Celia M T Greenwood
Journal:  Epigenetics       Date:  2017-04-07       Impact factor: 4.528

Review 5.  Metabolism as a key regulator in the pathogenesis of systemic lupus erythematosus.

Authors:  Yusuke Takeshima; Yukiko Iwasaki; Keishi Fujio; Kazuhiko Yamamoto
Journal:  Semin Arthritis Rheum       Date:  2019-04-25       Impact factor: 5.532

6.  Metabolic inflexibility: when mitochondrial indecision leads to metabolic gridlock.

Authors:  Deborah M Muoio
Journal:  Cell       Date:  2014-12-04       Impact factor: 41.582

7.  Mitochondrial DNA polymorphisms are associated with susceptibility and phenotype of systemic lupus erythematosus.

Authors:  A Jönsen; X Yu; L Truedsson; O Nived; G Sturfelt; S Ibrahim; Aa Bengtsson
Journal:  Lupus       Date:  2009-04       Impact factor: 2.911

8.  Chronic parvovirus B19 infection and systemic necrotising vasculitis: opportunistic infection or aetiological agent?

Authors:  T H Finkel; T J Török; P J Ferguson; E L Durigon; S R Zaki; D Y Leung; R J Harbeck; E W Gelfand; F T Saulsbury; J R Hollister
Journal:  Lancet       Date:  1994-05-21       Impact factor: 79.321

9.  Metabolic myopathy presenting with polyarteritis nodosa: a case report.

Authors:  Sahana Vishwanath; Mishal Abdullah; Amro Elbalkhi; Julian L Ambrus
Journal:  J Med Case Rep       Date:  2011-06-30

10.  Gastrointestinal disease in Sjogren's syndrome: related to food hypersensitivities.

Authors:  Christine Kim-Lee; Lakshmanan Suresh; Julian L Ambrus
Journal:  Springerplus       Date:  2015-12-12
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  1 in total

1.  [An unusual case of cardiomyopathy showing carnitine palmitoyltransferase deficiency].

Authors:  Imane Fetoui; Karima El Fakiri; Noureddine Rada; Ghizlane Draiss; Mohammed Bouskraoui
Journal:  Pan Afr Med J       Date:  2020-06-17
  1 in total

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