| Literature DB >> 32051586 |
Valérie Abadie1,2,3, Sangman M Kim4,5,6, Thomas Lejeune7,8, Brad A Palanski9, Jordan D Ernest4,5, Olivier Tastet10, Jordan Voisine4,5, Valentina Discepolo4, Eric V Marietta11,12,13, Mohamed B F Hawash10,14, Cezary Ciszewski4,5, Romain Bouziat4,5, Kaushik Panigrahi4, Irina Horwath11, Matthew A Zurenski4, Ian Lawrence4, Anne Dumaine10, Vania Yotova10, Jean-Christophe Grenier10, Joseph A Murray11, Chaitan Khosla9,15,16, Luis B Barreiro10,17,18, Bana Jabri19,20,21,22,23.
Abstract
Coeliac disease is a complex, polygenic inflammatory enteropathy caused by exposure to dietary gluten that occurs in a subset of genetically susceptible individuals who express either the HLA-DQ8 or HLA-DQ2 haplotypes1,2. The need to develop non-dietary treatments is now widely recognized3, but no pathophysiologically relevant gluten- and HLA-dependent preclinical model exists. Furthermore, although studies in humans have led to major advances in our understanding of the pathogenesis of coeliac disease4, the respective roles of disease-predisposing HLA molecules, and of adaptive and innate immunity in the development of tissue damage, have not been directly demonstrated. Here we describe a mouse model that reproduces the overexpression of interleukin-15 (IL-15) in the gut epithelium and lamina propria that is characteristic of active coeliac disease, expresses the predisposing HLA-DQ8 molecule, and develops villous atrophy after ingestion of gluten. Overexpression of IL-15 in both the epithelium and the lamina propria is required for the development of villous atrophy, which demonstrates the location-dependent central role of IL-15 in the pathogenesis of coeliac disease. In addition, CD4+ T cells and HLA-DQ8 have a crucial role in the licensing of cytotoxic T cells to mediate intestinal epithelial cell lysis. We also demonstrate a role for the cytokine interferon-γ (IFNγ) and the enzyme transglutaminase 2 (TG2) in tissue destruction. By reflecting the complex interaction between gluten, genetics and IL-15-driven tissue inflammation, this mouse model provides the opportunity to both increase our understanding of coeliac disease, and develop new therapeutic strategies.Entities:
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Year: 2020 PMID: 32051586 PMCID: PMC7047598 DOI: 10.1038/s41586-020-2003-8
Source DB: PubMed Journal: Nature ISSN: 0028-0836 Impact factor: 49.962