Literature DB >> 31939530

Fabry disease: genetics, pathology, and treatment.

Thaíza Passaglia Bernardes1, Renato Demarchi Foresto2, Gianna Mastroianni Kirsztajn1.   

Abstract

Fabry disease (FD) is a recessive monogenic inheritance disease linked to chromosome X, secondary to mutations in the GLA gene. Its prevalence is estimated between 1:8,454 and 1:117,000 among males and is probably underdiagnosed. Mutations in the GLA gene lead to the progressive accumulation of globotriaosylceramide (Gb3). Gb3 accumulates in lysosomes of different types of cells of the heart, kidneys, skin, eyes, central nervous system, and gastrointestinal system, and may lead to different clinical scenarios. The onset of symptoms occurs during childhood, with acroparesthesia, heat intolerance, and gastrointestinal symptoms, such as nausea, vomiting, abdominal pain, and neuropathic pain. Subsequently, symptoms related to progressive impairment appear, such as angiokeratomas, cornea verticillata, left ventricular hypertrophy, myocardial fibrosis, proteinuria, and renal insufficiency. The latter being the main cause of death in FD. The gold standard for diagnosis is the genetic analysis in search of mutation, in addition to family history. In homozygous patients, the enzyme activity can also be used. Once the diagnosis is confirmed, the patient and their family should receive genetic counseling. The treatment, in turn, currently focuses mainly on replacing the enzyme that is absent or deficient by means of enzyme replacement therapy, with the purpose of avoiding or removing deposits of Gb3. Chaperones can also be used for the treatment of some cases. It is considered that the specific treatment should be initiated as soon as a diagnosis is obtained, which can change the prognosis of the disease.

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Year:  2020        PMID: 31939530     DOI: 10.1590/1806-9282.66.S1.10

Source DB:  PubMed          Journal:  Rev Assoc Med Bras (1992)        ISSN: 0104-4230            Impact factor:   1.209


  7 in total

1.  Drug Repositioning for Fabry Disease: Acetylsalicylic Acid Potentiates the Stabilization of Lysosomal Alpha-Galactosidase by Pharmacological Chaperones.

Authors:  Maria Monticelli; Ludovica Liguori; Mariateresa Allocca; Andrea Bosso; Giuseppina Andreotti; Jan Lukas; Maria Chiara Monti; Elva Morretta; Maria Vittoria Cubellis; Bruno Hay Mele
Journal:  Int J Mol Sci       Date:  2022-05-04       Impact factor: 6.208

2.  Fabry's Disease: The Utility of a Multidisciplinary Screening Approach.

Authors:  Marco Angelo Monte; Massimiliano Veroux; Margherita Stefania Rodolico; Valentina Losi; Luigi Di Pino; Rita Bella; Giuseppe Lanza; Ines Paola Monte
Journal:  Life (Basel)       Date:  2022-04-22

Review 3.  Cutaneous pain in disorders affecting peripheral nerves.

Authors:  Cheryl L Stucky; Alexander R Mikesell
Journal:  Neurosci Lett       Date:  2021-10-01       Impact factor: 3.046

Review 4.  Stroke and Fabry Disease: A Review of Literature.

Authors:  Vinayak Mishra; Amit Banerjee; Arohi B Gandhi; Ifrah Kaleem; Josh Alexander; Mohamed Hisbulla; Vishmita Kannichamy; Sharathshiva Valaiyaduppu Subas; Pousette Hamid
Journal:  Cureus       Date:  2020-12-14

5.  Skin manifestations associated with systemic diseases - Part II.

Authors:  Juliana Martins Leal; Gabriela Higino de Souza; Paula Figueiredo de Marsillac; Alexandre Carlos Gripp
Journal:  An Bras Dermatol       Date:  2021-09-17       Impact factor: 1.896

6.  Galactomannan-Decorated Lipidic Nanocarrier for Gene Supplementation Therapy in Fabry Disease.

Authors:  Julen Rodríguez-Castejón; Itziar Gómez-Aguado; Marina Beraza-Millor; María Ángeles Solinís; Ana Del Pozo-Rodríguez; Alicia Rodríguez-Gascón
Journal:  Nanomaterials (Basel)       Date:  2022-07-08       Impact factor: 5.719

7.  α-Galactosidase A Augmentation by Non-Viral Gene Therapy: Evaluation in Fabry Disease Mice.

Authors:  Julen Rodríguez-Castejón; Ana Alarcia-Lacalle; Itziar Gómez-Aguado; Mónica Vicente-Pascual; María Ángeles Solinís Aspiazu; Ana Del Pozo-Rodríguez; Alicia Rodríguez-Gascón
Journal:  Pharmaceutics       Date:  2021-05-21       Impact factor: 6.321

  7 in total

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