Literature DB >> 31678403

Inhibitory designer receptors aggravate memory loss in a mouse model of down syndrome.

Eric D Hamlett1, Aurélie Ledreux2, Anah Gilmore2, Elena M Vazey3, Gary Aston-Jones4, Heather A Boger5, Daniel Paredes2, Ann-Charlotte E Granholm2.   

Abstract

The pontine nucleus locus coeruleus (LC) is the primary source of noradrenergic (NE) projections to the brain and is important for working memory, attention, and cognitive flexibility. Individuals with Down syndrome (DS) develop Alzheimer's disease (AD) with high penetrance and often exhibit working memory deficits coupled with degeneration of LC-NE neurons early in the progression of AD pathology. Designer receptors exclusively activated by designer drugs (DREADDs) are chemogenetic tools that allow targeted manipulation of discrete neuronal populations in the brain without the confounds of off-target effects. We utilized male Ts65Dn mice (a mouse model for DS), and male normosomic (NS) controls to examine the effects of inhibitory DREADDs delivered via an AAV vector under translational control of the synthetic PRSx8, dopamine β hydroxylase (DβH) promoter. This chemogenetic tool allowed LC inhibition upon administration of the inert DREADD ligand, clozapine-N-oxide (CNO). DREADD-mediated LC inhibition impaired performance in a novel object recognition task and reversal learning in a spatial task. DREADD-mediated LC inhibition gave rise to an elevation of α-adrenoreceptors both in NS and in Ts65Dn mice. Further, microglial markers showed that the inhibitory DREADD stimulation led to increased microglial activation in the hippocampus in Ts65Dn but not in NS mice. These findings strongly suggest that LC signaling is important for intact memory and learning in Ts65Dn mice and disruption of these neurons leads to increased inflammation and dysregulation of adrenergic receptors.
Copyright © 2019. Published by Elsevier Inc.

Entities:  

Keywords:  Alzheimer's disease; Designer receptors exclusively activated by designer drugs (DREADD); Down syndrome; Locus Coeruleus; Memory; Neuroinflammation; Norepinephrine

Mesh:

Substances:

Year:  2019        PMID: 31678403      PMCID: PMC7722242          DOI: 10.1016/j.nbd.2019.104616

Source DB:  PubMed          Journal:  Neurobiol Dis        ISSN: 0969-9961            Impact factor:   5.996


  90 in total

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Journal:  Brain Dev       Date:  2005-06       Impact factor: 1.961

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Review 3.  Cognitive Impairment, Neuroimaging, and Alzheimer Neuropathology in Mouse Models of Down Syndrome.

Authors:  Eric D Hamlett; Heather A Boger; Aurélie Ledreux; Christy M Kelley; Elliott J Mufson; Maria F Falangola; David N Guilfoyle; Ralph A Nixon; David Patterson; Nathan Duval; Ann-Charlotte E Granholm
Journal:  Curr Alzheimer Res       Date:  2016       Impact factor: 3.498

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Journal:  Nat Genet       Date:  1995-10       Impact factor: 38.330

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6.  Norepinephrine and neural plasticity: the effects of xylamine on experience-induced changes in brain weight, memory, and behavior.

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7.  Behavioral validation of the Ts65Dn mouse model for Down syndrome of a genetic background free of the retinal degeneration mutation Pde6b(rd1).

Authors:  Alberto C S Costa; Melissa R Stasko; Cecilia Schmidt; Muriel T Davisson
Journal:  Behav Brain Res       Date:  2009-08-29       Impact factor: 3.332

8.  Age-related neurodegeneration and memory loss in down syndrome.

Authors:  Jason P Lockrow; Ashley M Fortress; Ann-Charlotte E Granholm
Journal:  Curr Gerontol Geriatr Res       Date:  2012-03-20

9.  ImageJ2: ImageJ for the next generation of scientific image data.

Authors:  Curtis T Rueden; Johannes Schindelin; Mark C Hiner; Barry E DeZonia; Alison E Walter; Ellen T Arena; Kevin W Eliceiri
Journal:  BMC Bioinformatics       Date:  2017-11-29       Impact factor: 3.169

10.  Aging rather than aneuploidy affects monoamine neurotransmitters in brain regions of Down syndrome mouse models.

Authors:  Alain D Dekker; Yannick Vermeiren; Christelle Albac; Eva Lana-Elola; Sheona Watson-Scales; Dorota Gibbins; Tony Aerts; Debby Van Dam; Elizabeth M C Fisher; Victor L J Tybulewicz; Marie-Claude Potier; Peter P De Deyn
Journal:  Neurobiol Dis       Date:  2017-06-15       Impact factor: 5.996

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  3 in total

Review 1.  Rodent Modeling of Alzheimer's Disease in Down Syndrome: In vivo and ex vivo Approaches.

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Journal:  Front Neurosci       Date:  2022-06-07       Impact factor: 5.152

2.  Building the Future Therapies for Down Syndrome: The Third International Conference of the T21 Research Society.

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Journal:  Mol Syndromol       Date:  2021-05-20

3.  Metabolic correlates of prevalent mild cognitive impairment and Alzheimer's disease in adults with Down syndrome.

Authors:  Mark Mapstone; Thomas J Gross; Fabio Macciardi; Amrita K Cheema; Melissa Petersen; Elizabeth Head; Benjamin L Handen; William E Klunk; Bradley T Christian; Wayne Silverman; Ira T Lott; Nicole Schupf
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  3 in total

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