Literature DB >> 31639430

Multiple genetic mutations implicate spectrum of phenotypes in Bardet-Biedl syndrome.

Sanjiban Chakrabarty1, Swheta B Savantre2, C Ramachandra Bhat2, Kapaettu Satyamoorthy3.   

Abstract

Bardet-Biedl syndrome (BBS) is a clinically and genetically heterogeneous ciliopathy with several clinical features including retinitis pigmentosa, obesity, kidney dysfunction, postaxial polydactyly, behavioral dysfunction and hypogonadism with wide spectrum of additional features. With multiple phenotypes and heterogeneous distribution, it is unlikely that BBS is caused by single gene defect. We have performed clinical and genetic diagnosis of two individuals from an Indian family with classical BBS symptoms. Whole exome sequencing identified homozygous missense mutation in BBS10 gene, hemizygous missense AR and homozygous missense PDE6B mutations in the proband and affected sibling with BBS. Identification of BBS10 mutation along with AR and PDE6B gene mutation will expand the genetic and phenotypic spectrum in individuals with BBS.
Copyright © 2019 Elsevier B.V. All rights reserved.

Entities:  

Keywords:  AR; BBS; Bardet–Biedl syndrome; Hypogonadism; PDE6B; Retinitis pigmentosa

Year:  2019        PMID: 31639430     DOI: 10.1016/j.gene.2019.144164

Source DB:  PubMed          Journal:  Gene        ISSN: 0378-1119            Impact factor:   3.688


  3 in total

1.  Identification of a Novel Homozygous Mutation in BBS10 Gene in an Iranian Family with Bardet-Biedl Syndrome.

Authors:  Mohammad Dehani; Davood Zare-Abdollahi; Ata Bushehri; Azadeh Dehghani; Jalil Effati; Seyed Ali Mohammad Miratashi; Hamid Reza Khorram Khorshid
Journal:  Avicenna J Med Biotechnol       Date:  2021 Oct-Dec

2.  Ophthalmic and Genetic Features of Bardet Biedl Syndrome in a German Cohort.

Authors:  Fadi Nasser; Susanne Kohl; Anne Kurtenbach; Melanie Kempf; Saskia Biskup; Theresia Zuleger; Tobias B Haack; Nicole Weisschuh; Katarina Stingl; Eberhart Zrenner
Journal:  Genes (Basel)       Date:  2022-07-08       Impact factor: 4.141

3.  Allelic overload and its clinical modifier effect in Bardet-Biedl syndrome.

Authors:  Irene Perea-Romero; Carlos Solarat; Fiona Blanco-Kelly; Iker Sanchez-Navarro; Brais Bea-Mascato; Eduardo Martin-Salazar; Isabel Lorda-Sanchez; Saoud Tahsin Swafiri; Almudena Avila-Fernandez; Inmaculada Martin-Merida; Maria Jose Trujillo-Tiebas; Ester Carreño; Belen Jimenez-Rolando; Blanca Garcia-Sandoval; Pablo Minguez; Marta Corton; Diana Valverde; Carmen Ayuso
Journal:  NPJ Genom Med       Date:  2022-07-14       Impact factor: 6.083

  3 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.