| Literature DB >> 31372978 |
Boyang Sun1, Feng Xue1, Ying Feng2, Jing Sun3, Ziqiang Yu4, Ming Hou5, Jingyu Zhang6, Xiaojing Zeng7, Yongqiang Zhao8, Shimei Lian9, Meijuan Huang10, Ting Niu11, Zhongguang Cui12, Jingsheng Wu13, Renchi Yang1.
Abstract
Acquired haemophilia A (AHA) is a rare haemorrhagic disorder caused by autoantibodies directed against the functional epitopes of coagulation factor VIII (FVIII). Its management relies on prompt diagnosis, control of bleeding and eradication of the inhibitor by immunosuppression. China Acquired Hemophilia Registry (CARE), a nationwide multicentre registry, was intended to survey the status of AHA and standardize its diagnosis and therapy in China. One hundred and eighty-seven registered patients had an average age of 52 years. Diagnosis was delayed in 46·5% patients. There was a significant delay from diagnosis to immunosuppressive therapy in 68·3% patients. Bleeding control was significantly higher in patients treated with prothrombin complex concentrate (PCC) versus FVIII replacement therapy (84·6% vs. 34·4%; P < 0·001). Inhibitor eradication with a combination of steroids and cyclophosphamide showed a higher partial remission (PR) rate (92·2% vs. 70·3%) and stable complete remission (CR) rate (82·8% vs. 48·6%) than with steroids alone. Logistic regression model showed age and malignancy were significantly related to survival at final follow-up. The mean age for the survivors [51 years (IQR, 35-65 years)] was significantly lower than that of the non-survivors [79 years (IQR, 67-86 years)] (P < 0·001). Overall survival was higher in non-malignancy group than malignancy group (94·9% vs. 70%) (OR = 1·313; 95% CI, 0·913-1·889, P = 0·015).Entities:
Keywords: acquired haemophilia A; diagnosis; haemostatic treatment; immunosuppression; outcome; registry
Year: 2019 PMID: 31372978 DOI: 10.1111/bjh.16128
Source DB: PubMed Journal: Br J Haematol ISSN: 0007-1048 Impact factor: 6.998