Literature DB >> 31177193

Management of a case of orbital lymphangioma presenting in adulthood with negative-pressure aspiration and bleomycin injection.

Sagnik Sen1, Pallavi Singh1, Mandeep S Bajaj1, Nripen Gaur1.   

Abstract

We hereby report a case of a 55-year-old woman, with complaints of sudden onset outward protrusion of left eye progressing over 2 months, along with pain and loss of vision. Visual acuity in the affected eye was light perception only. On imaging, a well-defined solitary cystic lesion was noted in the retrobulbar space, which showed no enhancement on contrast-enhanced MRI. We performed fluid aspiration from the cyst under negative pressure and injected bleomycin as a sclerosant, without attempting a surgical excision. The proptosis reduced visibly, and after a week, visual acuity improved to finger counting at 1 m. At the 6 months follow-up, the patient did not show any recurrence of proptosis. This report highlights the importance of sclerosant therapy without the need for surgical excision in managing macrocystic lymphangiomas in adult age group. © BMJ Publishing Group Limited 2019. No commercial re-use. See rights and permissions. Published by BMJ.

Entities:  

Keywords:  eye; ophthalmology; therapeutic indications

Mesh:

Substances:

Year:  2019        PMID: 31177193      PMCID: PMC6557371          DOI: 10.1136/bcr-2018-227697

Source DB:  PubMed          Journal:  BMJ Case Rep        ISSN: 1757-790X


  17 in total

1.  Successful treatment of orbital lymphangioma with intralesional bleomycin and application of continuous negative pressure.

Authors:  Ka Hyun Lee; Sun Hyup Han; Jin Sook Yoon
Journal:  Korean J Ophthalmol       Date:  2015-02

2.  Correlation of surgical outcome with neuroimaging findings in periocular lymphangiomas.

Authors:  Kaan Gündüz; Sibel Demirel; Banu Yagmurlu; Esra Erden
Journal:  Ophthalmology       Date:  2006-05-26       Impact factor: 12.079

3.  Percutaneous drainage and ablation as first line therapy for macrocystic and microcystic orbital lymphatic malformations.

Authors:  Robert H Hill; William E Shiels; Jill A Foster; Craig N Czyz; Andrew Stacey; Kelly R Everman; Kenneth V Cahill
Journal:  Ophthalmic Plast Reconstr Surg       Date:  2012 Mar-Apr       Impact factor: 1.746

4.  Orbital venous-lymphatic malformations (lymphangiomas) mimicking cavernous hemangiomas.

Authors:  D Selva; D Strianese; G Bonavolonta; J Rootman
Journal:  Am J Ophthalmol       Date:  2001-03       Impact factor: 5.258

5.  Symposium: Tumors of the lids and orbit.

Authors: 
Journal:  Ophthalmology       Date:  1979-05       Impact factor: 12.079

6.  Orbital lymphangioma: an analysis of 26 patients.

Authors:  M Tunç; E Sadri; D H Char
Journal:  Br J Ophthalmol       Date:  1999-01       Impact factor: 4.638

7.  Surgical management, outcomes, and recurrence rate of orbital lymphangiomas.

Authors:  Jonathan J Russin; Leonardo Rangel-Castilla; M Yashar S Kalani; Robert F Spetzler
Journal:  J Clin Neurosci       Date:  2015-03-18       Impact factor: 1.961

8.  Sclerotherapy treatment of orbital lymphatic malformations: a large single-centre experience.

Authors:  Alex M Barnacle; Maria Theodorou; Sarah J Maling; Yassir Abou-Rayyah
Journal:  Br J Ophthalmol       Date:  2015-06-17       Impact factor: 4.638

9.  Bleomycin therapy for cystic hygroma.

Authors:  J Orford; A Barker; S Thonell; P King; J Murphy
Journal:  J Pediatr Surg       Date:  1995-09       Impact factor: 2.545

10.  Orbital lymphangioma. Correlation of magnetic resonance images and intraoperative findings.

Authors:  M Kazim; J S Kennerdell; W Rothfus; M Marquardt
Journal:  Ophthalmology       Date:  1992-10       Impact factor: 12.079

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