Literature DB >> 31028654

Intron retention is among six unreported AGL mutations identified in Malaysian GSD III patients.

Ili Syazwana Abdullah1, Ser-Huy Teh1, Fiqri Dizar Khaidizar2, Lock-Hock Ngu3, Wee-Teik Keng3, Sufin Yap4,5, Zulqarnain Mohamed6,7.   

Abstract

BACKGROUND: Glycogen storage disease type III is an autosomal recessive disorder that is caused by deficiencies of the glycogen debranching enzyme. Mutations within the AGL gene have been found to be heterogeneous, with some common mutations being reported in certain populations. The mutation spectrum of AGL gene in the multi-ethnic Malaysian population is still unknown.
OBJECTIVE: The present study seeks to determine the mutation spectrum of the AGL gene in Malaysian population.
METHODS: A total of eleven patients (eight Malay, two Chinese and one Bajau) were investigated. Genomic DNA was extracted and subsequently the AGL gene was amplified using specific primers and sequenced. Mutations found were screened in 150 healthy control samples either by restriction enzyme digestion assay or TaqMan® SNP Genotyping assay.
RESULTS: We identified six unreported mutations (c.1423+1G>T, c.2914_2915delAA, c.3814_3815delAG, c.4333T>G, c.4490G>A, c.4531_4534delTGTC) along with three previously reported mutations (c.99C>T, c.1783C>T, c.2681+1G>A). One of the six unreported mutation causes abnormal splicing and results in retention of intron 12 of the mature transcript, while another is a termination read-through. One of the reported mutation c.2681+1G>A was recurrently found in the Malay patients (n = 7 alleles; 31.8%).
CONCLUSION: The mutation spectrum of the AGL gene in Malaysian patients has shown considerable heterogeneity, and all unreported mutations were absent in all 150 healthy control samples tested.

Entities:  

Keywords:  Catalytic domain; Glycogen debranching enzyme; Glycogen storage disease type III; Mutant proteins; Mutation

Mesh:

Substances:

Year:  2019        PMID: 31028654     DOI: 10.1007/s13258-019-00815-9

Source DB:  PubMed          Journal:  Genes Genomics        ISSN: 1976-9571            Impact factor:   1.839


  17 in total

1.  Glycogen storage disease type III (glycogen debranching enzyme deficiency): correlation of biochemical defects with myopathy and cardiomyopathy.

Authors:  R A Coleman; H S Winter; B Wolf; J M Gilchrist; Y T Chen
Journal:  Ann Intern Med       Date:  1992-06-01       Impact factor: 25.391

2.  Glycogen storage disease type IIIa: first report of a causative missense mutation (G1448R) of the glycogen debranching enzyme gene found in a homozygous patient.

Authors:  M Okubo; F Kanda; A Horinishi; K Takahashi; S Okuda; K Chihara; T Murase
Journal:  Hum Mutat       Date:  1999-12       Impact factor: 4.878

3.  Molecular genetic basis and prevalence of glycogen storage disease type IIIA in the Faroe Islands.

Authors:  R Santer; M Kinner; U Steuerwald; S Kjaergaard; F Skovby; H Simonsen; W L Shaiu; Y T Chen; R Schneppenheim; J Schaub
Journal:  Eur J Hum Genet       Date:  2001-05       Impact factor: 4.246

4.  A mutation analysis of the AGL gene in Korean patients with glycogen storage disease type III.

Authors:  Jae Sung Ko; Jin Soo Moon; Jeong Kee Seo; Hye Ran Yang; Ju Young Chang; Sung Sup Park
Journal:  J Hum Genet       Date:  2013-11-21       Impact factor: 3.172

5.  A novel point mutation in an acceptor splice site of intron 32 (IVS32 A-12-->G) but no exon 3 mutations in the glycogen debranching enzyme gene in a homozygous patient with glycogen storage disease type IIIb.

Authors:  M Okubo; A Horinishi; N Nakamura; Y Aoyama; M Hashimoto; Y Endo; T Murase
Journal:  Hum Genet       Date:  1998-01       Impact factor: 4.132

6.  A nonsense mutation due to a single base insertion in the 3'-coding region of glycogen debranching enzyme gene associated with a severe phenotype in a patient with glycogen storage disease type IIIa.

Authors:  J Shen; Y Bao; Y T Chen
Journal:  Hum Mutat       Date:  1997       Impact factor: 4.878

Review 7.  Molecular characterization of glycogen storage disease type III.

Authors:  J J Shen; Y T Chen
Journal:  Curr Mol Med       Date:  2002-03       Impact factor: 2.222

8.  Molecular features of 23 patients with glycogen storage disease type III in Turkey: a novel mutation p.R1147G associated with isolated glucosidase deficiency, along with 9 AGL mutations.

Authors:  Yoshiko Aoyama; Isil Ozer; Mubeccel Demirkol; Tetsu Ebara; Toshio Murase; Teodor Podskarbi; Yoon S Shin; Gulden Gokcay; Minoru Okubo
Journal:  J Hum Genet       Date:  2009-10-16       Impact factor: 3.172

9.  Molecular analysis of the AGL gene: identification of 25 novel mutations and evidence of genetic heterogeneity in patients with Glycogen Storage Disease Type III.

Authors:  Jennifer L Goldstein; Stephanie L Austin; Keri Boyette; Angela Kanaly; Aravind Veerapandiyan; Catherine Rehder; Priya S Kishnani; Deeksha S Bali
Journal:  Genet Med       Date:  2010-07       Impact factor: 8.822

10.  Peroxisomal lactate dehydrogenase is generated by translational readthrough in mammals.

Authors:  Fabian Schueren; Thomas Lingner; Rosemol George; Julia Hofhuis; Corinna Dickel; Jutta Gärtner; Sven Thoms
Journal:  Elife       Date:  2014-09-23       Impact factor: 8.140

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Authors:  Gudrun Wahlström; Samuel Heron; Matias Knuuttila; Elina Kaikkonen; Nea Tulonen; Olli Metsälä; Christoffer Löf; Otto Ettala; Peter J Boström; Pekka Taimen; Matti Poutanen; Johanna Schleutker
Journal:  Hum Mol Genet       Date:  2022-06-22       Impact factor: 5.121

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