Literature DB >> 30993645

CADASIL with Atypical Clinical Symptoms, Magnetic Resonance Imaging, and Novel Mutations: Two Case Reports and a Review of the Literature.

U Serpil Sari1, Aysin Kisabay2, Melike Batum3, Serdar Tarhan4, Nihal Dogan2, Aysun Coskunoglu5, Sirri Cam5, Hikmet Yilmaz2, Deniz Selcuki2.   

Abstract

Cerebral autosomal dominant arteriopathy with subcortical infarcts and leukoencephalopathy (CADASIL) is a hereditary microangiopathy with adult onset caused by a missense mutation in the NOTCH3 gene in chromosome 19p13. It presents with autosomal dominant arteriopathy, subcortical infarctions, and leukoencephalopathy. Its common clinical presentations are seen as recurrent strokes, migraine or migraine-like headaches, progressive dementia, pseudobulbar paralysis, and psychiatric conditions. Two patients with CADASIL syndrome, whose diagnosis was made based on clinical course, age of onset, imaging findings, and genetic assays in the patients and family members, are presented here because of new familial polymorphisms. The first patient, with cerebellar and psychotic findings, had widespread non-confluent hyperintense lesions as well as moderate cerebellar atrophy in cranial magnetic resonance scanning. The other patient, with headache, dizziness, and forgetfulness, had gliotic lesions in both cerebral hemispheres. CADASIL gene studies revealed a new polymorphism in exon 33 in the first patient. In the other patient, the NOTCH3 gene was identified as a new variant of p.H243P (c.728A > C heterozygous). By reporting a family presenting with various clinical symptoms in the presence of new polymorphisms, we emphasize that CADASIL syndrome may present with various clinical courses and should be considered in differential diagnoses.

Entities:  

Keywords:  CADASIL; Genetic testing; Headache; MRI; NOTCH3; Small vessel disease

Year:  2019        PMID: 30993645     DOI: 10.1007/s12031-019-01313-z

Source DB:  PubMed          Journal:  J Mol Neurosci        ISSN: 0895-8696            Impact factor:   3.444


  4 in total

1.  Ataxia Associated with CADASIL: a Pathology-Confirmed Case Report and Literature Review.

Authors:  Don Gueu Park; Je Hong Min; Seong Hyang Sohn; Young Bae Sohn; Jung Han Yoon
Journal:  Cerebellum       Date:  2020-12       Impact factor: 3.847

2.  Prevalence and Atypical Clinical Characteristics of NOTCH3 Mutations Among Patients Admitted for Acute Lacunar Infarctions.

Authors:  Takashi Okada; Kazuo Washida; Kenichi Irie; Satoshi Saito; Michio Noguchi; Tsutomu Tomita; Masatoshi Koga; Kazunori Toyoda; Shuhei Okazaki; Takashi Koizumi; Ikuko Mizuta; Toshiki Mizuno; Masafumi Ihara
Journal:  Front Aging Neurosci       Date:  2020-05-14       Impact factor: 5.750

3.  Mutations in NOTCH3 Gene may Promote the Clinical Presentation of Spinocerebellar Ataxia Type 37 Caused by Mutations in DAB1 Gene.

Authors:  Zhao-Wei Wang; Li-Ping Wang; Ye Du; Qi Liu
Journal:  Front Mol Biosci       Date:  2021-06-16

Review 4.  Monogenic Causes of Strokes.

Authors:  Justyna Chojdak-Łukasiewicz; Edyta Dziadkowiak; Sławomir Budrewicz
Journal:  Genes (Basel)       Date:  2021-11-23       Impact factor: 4.096

  4 in total

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