Literature DB >> 30769148

Structure of G57W mutant of human γS-crystallin and its involvement in cataract formation.

Khandekar Jishan Bari1, Shrikant Sharma1, Kandala V R Chary2.   

Abstract

A recently identified mutant of human γS-crystallin, G57W is associated with dominant congenital cataracts, the familial determinate of childhood blindness worldwide. To investigate the structural and functional changes that mediate the effect of this cataract-related mutant to compromise eye lens transparency and cause lens opacification in children, we recently reported complete sequence-specific resonance assignments of γS-G57W using a suite of heteronuclear NMR experiments. As a follow up, we have determined the 3D structure of γS-G57W and studied its conformational dynamics by solution NMR spectroscopy. Our structural dynamics results reveal greater flexibility of the N-terminal domain, which undergoes site-specific structural changes to accommodate W57, than its C-terminal counterpart. Our structural inferences that the unusual solvent exposure of W57 is associated with rearrangement of the N-terminal domain suggest an efficient pathway for increased aggregation in γS-G57W and illuminates the molecular dynamics underlying cataractogenic aggregation of lens crystallins in particular and aggregation of proteins in general.
Copyright © 2019 Elsevier Inc. All rights reserved.

Entities:  

Keywords:  3D structure; Aggregation propensity; Conformational dynamics; Congenital cataract

Mesh:

Substances:

Year:  2019        PMID: 30769148     DOI: 10.1016/j.jsb.2019.02.003

Source DB:  PubMed          Journal:  J Struct Biol        ISSN: 1047-8477            Impact factor:   2.867


  5 in total

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3.  Biophysical Reviews' "Meet the Councilor Series"-a profile of Kandala V. R. Chary.

Authors:  Kandala V R Chary
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Authors:  Zhe-Kun Jia; Chen-Xi Fu; Ai-Ling Wang; Ke Yao; Xiang-Jun Chen
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Review 5.  Chemical Properties Determine Solubility and Stability in βγ-Crystallins of the Eye Lens.

Authors:  Megan A Rocha; Marc A Sprague-Piercy; Ashley O Kwok; Kyle W Roskamp; Rachel W Martin
Journal:  Chembiochem       Date:  2021-02-10       Impact factor: 3.164

  5 in total

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