Literature DB >> 30557270

Williams syndrome: recent advances in our understanding of cognitive, social and psychological functioning.

Rachel Royston1, Jane Waite2, Patricia Howlin3.   

Abstract

PURPOSE OF REVIEW: Since the last review of Williams syndrome in Current Opinion (2001) there have been many advances in knowledge about the cognitive, social and psychological impairments that characterize the disorder. The present review focuses on current research in these areas. RECENT
FINDINGS: Williams syndrome is associated with a wide range of cognitive, linguistic, social and other difficulties. When young, these deficits may appear relatively mild - for example, many children are highly sociable and talkative - but with age the impact of these difficulties becomes more evident. Thus, inappropriate social behaviours can significantly increase the risk of social exclusion and vulnerability to abuse. Their superficially good speech can lead to educational and other services failing to understand the true extent of impairments or the need for specialist support. Mental health problems, especially related to anxiety, often become an increasing challenge from adolescence onwards.
SUMMARY: The core difficulties associated with Williams syndrome have a cascading effect on many areas of development over time. However, specialist provision is rare and intervention trials are almost nonexistent. Longitudinal research is needed to identify factors associated with cognitive, social and emotional problems and to develop more effective ways of minimizing and treating difficulties.

Entities:  

Mesh:

Year:  2019        PMID: 30557270     DOI: 10.1097/YCO.0000000000000477

Source DB:  PubMed          Journal:  Curr Opin Psychiatry        ISSN: 0951-7367            Impact factor:   4.741


  6 in total

1.  Heritability of social behavioral phenotypes and preliminary associations with autism spectrum disorder risk genes in rhesus macaques: A whole exome sequencing study.

Authors:  Chris Gunter; R Alan Harris; Zsofia Kovacs-Balint; Muthuswamy Raveendran; Vasiliki Michopoulos; Jocelyne Bachevalier; Jessica Raper; Mar M Sanchez; Jeffrey Rogers
Journal:  Autism Res       Date:  2022-01-29       Impact factor: 4.633

2.  The Profiles and Correlates of Psychopathology in Adolescents and Adults with Williams, Fragile X and Prader-Willi Syndromes.

Authors:  R Royston; C Oliver; P Howlin; A Dosse; P Armitage; J Moss; J Waite
Journal:  J Autism Dev Disord       Date:  2020-03

3.  Atypical deletion of Williams-Beuren syndrome reveals the mechanism of neurodevelopmental disorders.

Authors:  Jianrong Zhou; Ying Zheng; Guiying Liang; Xiaoli Xu; Jian Liu; Shaoxian Chen; Tongkai Ge; Pengju Wen; Yong Zhang; Xiaoqing Liu; Jian Zhuang; Yueheng Wu; Jimei Chen
Journal:  BMC Med Genomics       Date:  2022-04-04       Impact factor: 3.063

4.  Cannabinoid signaling modulation through JZL184 restores key phenotypes of a mouse model for Williams-Beuren syndrome.

Authors:  Alba Navarro-Romero; Lorena Galera-López; Paula Ortiz-Romero; Alberto Llorente-Ovejero; Lucía de Los Reyes-Ramírez; Iker Bengoetxea de Tena; Anna Garcia-Elias; Aleksandra Mas-Stachurska; Marina Reixachs-Solé; Antoni Pastor; Rafael de la Torre; Rafael Maldonado; Begoña Benito; Eduardo Eyras; Rafael Rodríguez-Puertas; Victoria Campuzano; Andres Ozaita
Journal:  Elife       Date:  2022-10-11       Impact factor: 8.713

5.  Upregulated 5-HT1A receptor-mediated currents in the prefrontal cortex layer 5 neurons in the 15q11-13 duplication mouse model of autism.

Authors:  Fumihito Saitow; Toru Takumi; Hidenori Suzuki
Journal:  Mol Brain       Date:  2020-08-24       Impact factor: 4.041

6.  Pragmatic Profiles of Adults with Fragile X Syndrome and Williams Syndrome.

Authors:  Eliseo Diez-Itza; Aitana Viejo; Maite Fernández-Urquiza
Journal:  Brain Sci       Date:  2022-03-13
  6 in total

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