Literature DB >> 30354341

Healthcare Utilization and Patients' Perspectives After Receiving a Positive Genetic Test for Familial Hypercholesterolemia.

Laney K Jones1, Alanna Kulchak Rahm2, Kandamurugu Manickam2, Loren Butry2, Amanda Lazzeri2, Timothy Corcoran2, Daniel Komar2, Navya S Josyula3, Sarah A Pendergrass3, Amy C Sturm2, Michael F Murray2,4.   

Abstract

BACKGROUND: The MyCode Community Health Initiative (MyCode) is returning actionable results from whole exome sequencing. Familial hypercholesterolemia (FH) is an inherited condition characterized by premature cardiovascular disease.
METHODS: We used multiple methods to assess care in 28 MyCode participants who received FH results. Chart reviews were conducted on 23 individuals in the sample and 7 individuals participated semistructured interviews.
RESULTS: Chart reviews for 23 individuals with a Geisinger primary care provider found that 4 individuals (17% of 23) were at LDL-C (low-density lipoprotein cholesterol) goal (of either LDL-C <100 mg/dL for primary prevention and LDL-C <70 mg/dL for secondary prevention) and 17 individuals (74% of 23) were prescribed lipid-lowering therapy before genetic result disclosure. After disclosure of the genetic test result, 5 individuals (22% of 23) met their LDL-C goal and 18 individuals (78% of 23) were prescribed lipid-lowering therapy. Follow-up care about this result was not documented for 4 individuals (17% of 23). Changes to intensity of medication management were made for 8 individuals (47% of 17 individuals previously prescribed lipid-lowering therapy). Interviewed individuals (n=7) were not surprised by their result as all knew they had high cholesterol; however, individuals did not seem to discern FH as a separate condition from their high cholesterol.
CONCLUSIONS: Among individuals receiving genetic diagnosis of FH, >25% had no changes to lipid-lowering therapy, despite not being at LDL-C goal and learning their high cholesterol is related to a genetic condition requiring more aggressive treatment. Individuals and clinicians may have an inadequate understanding of FH as a distinct condition requiring enhanced medical management.

Entities:  

Keywords:  cardiovascular disease; disclosure; epidemiology; hypercholesterolemia, familial; whole exome sequencing

Mesh:

Substances:

Year:  2018        PMID: 30354341     DOI: 10.1161/CIRCGEN.118.002146

Source DB:  PubMed          Journal:  Circ Genom Precis Med        ISSN: 2574-8300


  11 in total

1.  Genetic Testing for Familial Hypercholesterolemia: Health Technology Assessment.

Authors: 
Journal:  Ont Health Technol Assess Ser       Date:  2022-08-23

2.  A RE-AIM Framework Analysis of DNA-Based Population Screening: Using Implementation Science to Translate Research Into Practice in a Healthcare System.

Authors:  Laney K Jones; Natasha T Strande; Evan M Calvo; Jingheng Chen; Gabriela Rodriguez; Cara Z McCormick; Miranda L G Hallquist; Juliann M Savatt; Heather Rocha; Marc S Williams; Amy C Sturm; Adam H Buchanan; Russell E Glasgow; Christa L Martin; Alanna Kulchak Rahm
Journal:  Front Genet       Date:  2022-05-25       Impact factor: 4.772

Review 3.  Familial hypercholesterolaemia: evolving knowledge for designing adaptive models of care.

Authors:  Gerald F Watts; Samuel S Gidding; Pedro Mata; Jing Pang; David R Sullivan; Shizuya Yamashita; Frederick J Raal; Raul D Santos; Kausik K Ray
Journal:  Nat Rev Cardiol       Date:  2020-01-23       Impact factor: 32.419

Review 4.  Barriers and Facilitators to Genetic Testing for Familial Hypercholesterolemia in the United States: A Review.

Authors:  Rachele M Hendricks-Sturrup; Kathleen M Mazor; Amy C Sturm; Christine Y Lu
Journal:  J Pers Med       Date:  2019-07-01

5.  Developing and Optimizing Innovative Tools to Address Familial Hypercholesterolemia Underdiagnosis: Identification Methods, Patient Activation, and Cascade Testing for Familial Hypercholesterolemia.

Authors:  Gemme Campbell-Salome; Laney K Jones; Max F Masnick; Nephi A Walton; Catherine D Ahmed; Adam H Buchanan; Andrew Brangan; Edward D Esplin; David G Kann; Ilene G Ladd; Melissa A Kelly; Iris Kindt; H Lester Kirchner; Mary P McGowan; Megan N McMinn; Ana Morales; Kelly D Myers; Matthew T Oetjens; Alanna Kulchak Rahm; Tara J Schmidlen; Amanda Sheldon; Emilie Simmons; Moran Snir; Natasha T Strande; Nicole L Walters; Katherine Wilemon; Marc S Williams; Samuel S Gidding; Amy C Sturm
Journal:  Circ Genom Precis Med       Date:  2021-01-22

6.  Association of the Interaction Between Familial Hypercholesterolemia Variants and Adherence to a Healthy Lifestyle With Risk of Coronary Artery Disease.

Authors:  Akl C Fahed; Minxian Wang; Aniruddh P Patel; Ezimamaka Ajufo; Dimitri J Maamari; Krishna G Aragam; Deanna G Brockman; Trish Vosburg; Patrick T Ellinor; Kenney Ng; Amit V Khera
Journal:  JAMA Netw Open       Date:  2022-03-01

7.  The return of individual genomic results to research participants: design and pilot study of Tohoku Medical Megabank Project.

Authors:  Hiroshi Kawame; Akimune Fukushima; Nobuo Fuse; Fuji Nagami; Yoichi Suzuki; Mika Sakurai-Yageta; Jun Yasuda; Yumi Yamaguchi-Kabata; Kengo Kinoshita; Soichi Ogishima; Takako Takai; Shinichi Kuriyama; Atsushi Hozawa; Naoki Nakaya; Tomohiro Nakamura; Naoko Minegishi; Junichi Sugawara; Kichiya Suzuki; Hiroaki Tomita; Akira Uruno; Tomoko Kobayashi; Yayoi Aizawa; Tomoharu Tokutomi; Kayono Yamamoto; Kinuko Ohneda; Shigeo Kure; Yoko Aoki; Hideki Katagiri; Yasushi Ishigaki; Shojiro Sawada; Makoto Sasaki; Masayuki Yamamoto
Journal:  J Hum Genet       Date:  2021-07-08       Impact factor: 3.172

8.  Enablers and barriers to treatment adherence in heterozygous familial hypercholesterolaemia: a qualitative evidence synthesis.

Authors:  Fiona J Kinnear; Elaine Wainwright; Rachel Perry; Fiona E Lithander; Graham Bayly; Alyson Huntley; Jennifer Cox; Julian Ph Shield; Aidan Searle
Journal:  BMJ Open       Date:  2019-07-31       Impact factor: 2.692

9.  Quantifying the polygenic contribution to variable expressivity in eleven rare genetic disorders.

Authors:  M T Oetjens; M A Kelly; A C Sturm; C L Martin; D H Ledbetter
Journal:  Nat Commun       Date:  2019-10-25       Impact factor: 14.919

10.  Clinical outcomes of a genomic screening program for actionable genetic conditions.

Authors:  Adam H Buchanan; H Lester Kirchner; Marci L B Schwartz; Melissa A Kelly; Tara Schmidlen; Laney K Jones; Miranda L G Hallquist; Heather Rocha; Megan Betts; Rachel Schwiter; Loren Butry; Amanda L Lazzeri; Lauren R Frisbie; Alanna Kulchak Rahm; Jing Hao; Huntington F Willard; Christa L Martin; David H Ledbetter; Marc S Williams; Amy C Sturm
Journal:  Genet Med       Date:  2020-06-30       Impact factor: 8.864

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.