Literature DB >> 30329211

A rare male patient with Fontaine progeroid syndrome caused by p.R217H de novo mutation in SLC25A24.

María Elena Rodríguez-García1, Francisco Javier Cotrina-Vinagre1, Jaime Cruz-Rojo2, Lucía Garzón-Lorenzo2, Patricia Carnicero-Rodríguez1, Jaime Sánchez-Del Pozo2, Francisco Martínez-Azorín1,3.   

Abstract

We report the clinical and genetic findings in a 15-year-old Spanish boy presenting prenatal and postnatal growth retardation, reduced subcutaneous adipose tissue, premature skin wrinkling, sparse hair, short distal phalanges with small nails, umbilical hernia, wide anterior fontanel, and normal cognitive and motor development. Exome sequencing uncovered a heterozygous mutation in SLC25A24 (NM_013386: c.650G>A: p.R217H) that encodes for the calcium-binding mitochondrial carrier protein SCaMC-1. This gain-of-function variant has been previously associated with Fontaine syndrome and Gorlin-Chaudhry-Moss syndrome, two entities that show overlapping features, and have been recently subsumed under the name Fontaine progeroid syndrome (FPS; MIM: 612289) in OMIM. Here, we describe the first male patient with genetically confirmed FPS who survives at least until adolescence.
© 2018 Wiley Periodicals, Inc.

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Keywords:  zzm321990SLC25A24; Fontaine progeroid syndrome; Fontaine syndrome; Gorlin-Chaudhry-Moss syndrome; mitochondria

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Year:  2018        PMID: 30329211     DOI: 10.1002/ajmg.a.40496

Source DB:  PubMed          Journal:  Am J Med Genet A        ISSN: 1552-4825            Impact factor:   2.802


  2 in total

1.  A 9-year-old Korean girl with Fontaine progeroid syndrome: a case report with further phenotypical delineation and description of clinical course during long-term follow-up.

Authors:  Jaehui Ryu; Jung Min Ko; Choong-Ho Shin
Journal:  BMC Med Genet       Date:  2019-11-27       Impact factor: 2.103

2.  Is Gorlin-Chaudhry-Moss syndrome associated with aortopathy?

Authors:  Juno Legué; Jules H M François; Carla S P van Rijswijk; Thomas J van Brakel
Journal:  Eur J Cardiothorac Surg       Date:  2020-09-01       Impact factor: 4.191

  2 in total

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