| Literature DB >> 30218783 |
Claire-Marie Rangon1, Anne-Laure Schang2, Juliette Van Steenwinckel1, Leslie Schwendimann1, Sophie Lebon1, Tingting Fu3, Libo Chen3, Veronique Beneton4, Nathalie Journiac1, Pierrette Young-Ten1, Thomas Bourgeois1, Johanna Maze1, Boris Matrot1, Ana A Baburamani5, Veena Supramaniam5, Carina Mallard6, Lionel Trottet4, A David Edwards5, Henrik Hagberg7, Bobbi Fleiss8, Jingjun Li9, Tsu Tshen Chuang9, Pierre Gressens10.
Abstract
Fifteen million babies are born preterm every year and a significant number suffer from permanent neurological injuries linked to white matter injury (WMI). A chief cause of preterm birth itself and predictor of the severity of WMI is exposure to maternal-fetal infection-inflammation such as chorioamnionitis. There are no neurotherapeutics for this WMI. To affect this healthcare need, the repurposing of drugs with efficacy in other white matter injury models is an attractive strategy. As such, we tested the efficacy of GSK247246, an H3R antagonist/inverse agonist, in a model of inflammation-mediated WMI of the preterm born infant recapitulating the main clinical hallmarks of human brain injury, which are oligodendrocyte maturation arrest, microglial reactivity, and hypomyelination. WMI is induced by mimicking the effects of maternal-fetal infection-inflammation and setting up neuroinflammation. We induce this process at the time in the mouse when brain development is equivalent to the human third trimester; postnatal day (P)1 through to P5 with i.p. interleukin-1β (IL-1β) injections. We initiated GSK247246 treatment (i.p at 7 mg/kg or 20 mg/kg) after neuroinflammation was well established (on P6) and it was administered twice daily through to P10. Outcomes were assessed at P10 and P30 with gene and protein analysis. A low dose of GSK247246 (7 mg/kg) lead to a recovery in protein expression of markers of myelin (density of Myelin Basic Protein, MBP & Proteolipid Proteins, PLP) and a reduction in macro- and microgliosis (density of ionising adaptor protein, IBA1 & glial fibrillary acid protein, GFAP). Our results confirm the neurotherapeutic efficacy of targeting the H3R for WMI seen in a cuprizone model of multiple sclerosis and a recently reported clinical trial in relapsing-remitting multiple sclerosis patients. Further work is needed to develop a slow release strategy for this agent and test its efficacy in large animal models of preterm infant WMI.Entities:
Keywords: Encephalopathy; Neuroinflammation; Neuroprotection; Oligodendrocyte; Prematurity
Mesh:
Substances:
Year: 2018 PMID: 30218783 DOI: 10.1016/j.bbi.2018.09.017
Source DB: PubMed Journal: Brain Behav Immun ISSN: 0889-1591 Impact factor: 7.217