| Literature DB >> 30209698 |
Feyza Nur Tuncer1, Sibel Aylin Ugur Iseri2, Zuhal Yapici3, Mahmut Demir4, Meryem Karaca5, Mustafa Calik6.
Abstract
Krabbe disease (KD) or globoid cell leukodystrophy is an autosomal recessive lysosomal storage disorder involving the white matter of the peripheral and the central nervous systems. It is caused by a deficiency of galactocerebrosidase enzyme activity. The most common manifestation is the classical early onset KD that leads to patient's loss before the age of 2. Herein, we report the evaluation of a consanguineous family with three affected children manifesting severe neurological findings that ended with death before the age of 2, in an attempt to provide genetic diagnosis to the family. One of the children underwent detailed physical and neurological examinations, including brain magnetic resonance imaging (MRI) and scalp electroencephalography (EEG) evaluations. GALC genetic testing on this child enabled identification of a novel homozygous variant (NM_000153.3: c.1394C>T; p.(Thr465Ile)), which confirmed diagnosis as KD. Familial segregation of this variant was performed by PCR amplification and Sanger sequencing that revealed the parents as heterozygous carriers. We believe this novel GALC variant will not only help in genetic counseling to this family but will also aid in identification of future KD cases.Entities:
Keywords: Consanguinity; GALC; Genetic analysis; Krabbe disease; Novel variation
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Year: 2018 PMID: 30209698 DOI: 10.1007/s10072-018-3556-2
Source DB: PubMed Journal: Neurol Sci ISSN: 1590-1874 Impact factor: 3.307