| Literature DB >> 30126926 |
Stefan J Siira1, Giulia Rossetti1, Tara R Richman1, Kara Perks1, Judith A Ermer1, Irina Kuznetsova1, Laetitia Hughes1, Anne-Marie J Shearwood1, Helena M Viola2, Livia C Hool2,3, Oliver Rackham1,4, Aleksandra Filipovska5,4.
Abstract
The molecular roles of the dually targeted ElaC domain protein 2 (ELAC2) during nuclear and mitochondrial RNA processing in vivo have not been distinguished. We generated conditional knockout mice of ELAC2 to identify that it is essential for life and its activity is non-redundant. Heart and skeletal muscle-specific loss of ELAC2 causes dilated cardiomyopathy and premature death at 4 weeks. Transcriptome-wide analyses of total RNAs, small RNAs, mitochondrial RNAs, and miRNAs identified the molecular targets of ELAC2 in vivo We show that ELAC2 is required for processing of tRNAs and for the balanced maintenance of C/D box snoRNAs, miRNAs, and a new class of tRNA fragments. We identify that correct biogenesis of regulatory non-coding RNAs is essential for both cytoplasmic and mitochondrial protein synthesis and the assembly of mitochondrial ribosomes and cytoplasmic polysomes. We show that nuclear tRNA processing is required for the balanced production of snoRNAs and miRNAs for gene expression and that 3' tRNA processing is an essential step in the production of all mature mitochondrial RNAs and the majority of nuclear tRNAs.Entities:
Keywords: RNA processing; RNA‐Seq; cardiomyopathy; non‐coding RNAs; snoRNAs
Mesh:
Substances:
Year: 2018 PMID: 30126926 PMCID: PMC6172459 DOI: 10.15252/embr.201846198
Source DB: PubMed Journal: EMBO Rep ISSN: 1469-221X Impact factor: 8.807