Literature DB >> 30115503

GLUT-1 deficiency presenting with seizures and reversible leukoencephalopathy on MRI imaging.

Naila Ismayilova1, Yael Hacohen1, Andrew D MacKinnon2, Frances Elmslie3, Antonia Clarke4.   

Abstract

Glucose transporter type 1 (GLUT1) deficiency syndrome is a well recognised genetic neurometabolic disorder typically presenting with progressive encephalopathy, acquired microcephaly and drug-resistant epilepsy. Imaging is normal in the majority. Here we describe a 5-month-old boy who presented with motor delay, myoclonic jerks and tonic-clonic seizures. His MRI brain scan revealed confluent symmetrical T2 hyperintense signal abnormality in both anterior frontal lobes and delayed myelination. Neurometabolic screen revealed low CSF glucose and lactate levels. A pathogenic de novo heterozygous mutation in SLC2A1 (c.275+1G > A) confirmed the diagnosis of GLUT1 deficiency. Ketogenic diet resulted in a dramatic termination of his seizures at 72 h. At 15 months, he continued to be seizure free with marked developmental catch up. Repeat imaging revealed a significant resolution of the previously seen changes. This case suggests that GLUT1 deficiency should be considered in the differential diagnosis of infants with suspected genetic leukoencephalopathies with important treatment implications.
Copyright © 2018. Published by Elsevier Ltd.

Entities:  

Keywords:  GLUT1 deficiency; Ketogenic diet; Leukoencephalopathy

Mesh:

Substances:

Year:  2018        PMID: 30115503     DOI: 10.1016/j.ejpn.2018.02.002

Source DB:  PubMed          Journal:  Eur J Paediatr Neurol        ISSN: 1090-3798            Impact factor:   3.140


  4 in total

Review 1.  Modulation of Glucose Availability and Effects of Hypo- and Hyperglycemia on Status Epilepticus: What We Do Not Know Yet?

Authors:  Igor Santana de Melo; Amanda Larissa Dias Pacheco; Yngrid Mickaelli Oliveira Dos Santos; Laura Mello Figueiredo; Dannyele Cynthia Santos Pimentel Nicacio; Leia Cardoso-Sousa; Marcelo Duzzioni; Daniel Leite Góes Gitaí; Cristiane Queixa Tilelli; Robinson Sabino-Silva; Olagide Wagner de Castro
Journal:  Mol Neurobiol       Date:  2020-09-25       Impact factor: 5.590

Review 2.  Morphological and Advanced Imaging of Epilepsy: Beyond the Basics.

Authors:  Aikaterini Fitsiori; Shivaprakash Basavanthaiah Hiremath; José Boto; Valentina Garibotto; Maria Isabel Vargas
Journal:  Children (Basel)       Date:  2019-03-11

3.  Diagnostic and Clinical Manifestation Differences of Glucose Transporter Type 1 Deficiency Syndrome in a Family with SLC2A1 Gene Mutation.

Authors:  Weronika Pawlik; Patrycja Okulewicz; Jakub Pawlik; Elżbieta Krzywińska-Zdeb
Journal:  Int J Environ Res Public Health       Date:  2022-03-10       Impact factor: 3.390

4.  Re-analysis of whole-exome sequencing data reveals a novel splicing variant in the SLC2A1 in a patient with GLUT1 Deficiency Syndrome 1 accompanied by hemangioma: a case report.

Authors:  Tugce Bozkurt; Yasemin Alanay; Ugur Isik; Ugur Sezerman
Journal:  BMC Med Genomics       Date:  2021-07-31       Impact factor: 3.063

  4 in total

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