Literature DB >> 30031702

Prediction of Life-Threatening Ventricular Arrhythmia in Patients With Arrhythmogenic Cardiomyopathy: A Primary Prevention Cohort Study.

Øyvind H Lie1, Christine Rootwelt-Norberg2, Lars A Dejgaard1, Ida Skrinde Leren1, Mathis K Stokke1, Thor Edvardsen3, Kristina H Haugaa4.   

Abstract

OBJECTIVES: This study aimed to identify clinical, electrocardiographic (ECG) and cardiac imaging predictors of first-time life-threatening ventricular arrhythmia in patients with arrhythmogenic cardiomyopathy (AC).
BACKGROUND: The role of clinical, electrocardiographic, and cardiac imaging parameters in risk stratification of patients without ventricular arrhythmia is unclear.
METHODS: We followed consecutive AC probands and mutation-positive family members with no documented ventricular arrhythmia from time of diagnosis to first event. We assessed clinical, electrocardiographic, and cardiac imaging parameters according to Task Force Criteria of 2010 in addition to left ventricular (LV) and strain parameters. High-intensity exercise was defined as >6 metabolic equivalents.
RESULTS: We included 117 patients (29% probands, 50% female, age 40 ± 17 years). During 4.2 (interquartile range [IQR]: 2.4 to 7.4) years of follow-up, 18 (15%) patients experienced life-threatening ventricular arrhythmias. The 1-, 2-, and 5-year incidence was 6%, 9%, and 22%, respectively. History of high-intensity exercise, T-wave inversions ≥V3, and greater LV mechanical dispersion were the strongest risk markers (adjusted hazard ratio [HR]: 4.7 [95% confidence interval (CI): 1.2 to 17.5]; p = 0.02, 4.7 [95% CI: 1.6 to 13.9]; p = 0.005), and 1.4 [95% CI: 1.2 to 1.6] by 10-ms increments; p < 0.001, respectively). Median arrhythmia-free survival in patients with all risk factors was 1.2 (95% CI: 0.4 to 1.9) years, compared with an estimated 12.0 (95% CI: 11.5 to 12.5) years in patients without any risk factors.
CONCLUSIONS: History of high-intensity exercise, electrocardiographic T-wave inversions ≥V3, and greater LV mechanical dispersion were strong predictors of life-threatening ventricular arrhythmia. Patients without any of these risk factors had minimal risk, whereas ≥2 risk factors increased the risk dramatically. This may help to make decisions on primary preventive implantable cardioverter defibrillator (ICD) therapy.
Copyright © 2018 The Authors. Published by Elsevier Inc. All rights reserved.

Entities:  

Keywords:  ARVC; arrhythmogenic cardiomyopathy; prediction; strain echocardiography; ventricular arrhythmia

Mesh:

Year:  2018        PMID: 30031702     DOI: 10.1016/j.jcmg.2018.05.017

Source DB:  PubMed          Journal:  JACC Cardiovasc Imaging        ISSN: 1876-7591


  13 in total

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2.  Usefulness of echocardiography for predicting ventricular tachycardia detected by implantable loop recorder in syncope patients.

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Review 3.  Natural History of Arrhythmogenic Cardiomyopathy.

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5.  Sudden Cardiac Death Prediction in Arrhythmogenic Right Ventricular Cardiomyopathy: A Multinational Collaboration.

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Journal:  Circ Arrhythm Electrophysiol       Date:  2020-12-09

6.  Impact of pregnancy and risk factors for ventricular arrhythmias in women with tetralogy of Fallot.

Authors:  Alessia Quattrone; Oyvind H Lie; Eirik Nestaas; Charlotte de Lange; Kirsti Try; Harald L Lindberg; Helge Skulstad; Gunnar Erikssen; Thor Edvardsen; Kristina Haugaa; Mette E Estensen
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7.  Clinical Findings and Diagnostic Yield of Arrhythmogenic Cardiomyopathy Through Genomic Screening of Pathogenic or Likely Pathogenic Desmosome Gene Variants.

Authors:  Eric D Carruth; Dominik Beer; Amro Alsaid; Marci L B Schwartz; Megan McMinn; Melissa A Kelly; Adam H Buchanan; Christopher D Nevius; Hugh Calkins; Cynthia A James; Brittney Murray; Crystal Tichnell; Martin E Matsumura; H Lester Kirchner; Brandon K Fornwalt; Amy C Sturm; Christopher M Haggerty
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8.  Right Ventricular Strain Predicts Structural Disease Progression in Patients With Arrhythmogenic Right Ventricular Cardiomyopathy.

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9.  High penetrance and similar disease progression in probands and in family members with arrhythmogenic cardiomyopathy.

Authors:  Monica Chivulescu; Øyvind H Lie; Bogdan A Popescu; Helge Skulstad; Thor Edvardsen; Ruxandra O Jurcut; Kristina H Haugaa
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Review 10.  Mechanotransduction and Adrenergic Stimulation in Arrhythmogenic Cardiomyopathy: An Overview of in vitro and in vivo Models.

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