| Literature DB >> 30031565 |
H Lu2, H Lu2, J Vaucher3, C Tran4, P Vollenweider3, J Castioni3.
Abstract
Thiamine-responsive megaloblastic anemia (TRMA), also known as Rogers syndrome, is a rare autosomal recessive disease characterized by three main components: megaloblastic anemia, diabetes mellitus and sensorineural deafness. Those features occur in infancy but may arise during adolescence. Diagnosis relies on uncovering genetic variations (alleles) in the SLC19A2 gene, encoding for a high affinity thiamine transporter. This transporter is essentially present in hematopoietic stem cells, pancreatic beta cells and inner ear cells, explaining the clinical manifestations of the disease. Based on a multidisciplinary approach, treatment resides on lifelong thiamine oral supplementation at pharmacological doses, which reverses anemia and may delay development of diabetes. However, thiamine supplementation does not alleviate already existing hearing defects.Entities:
Keywords: Analyse de mutations d’ADN; Anémie mégaloblastique; Carence en thiamine; DNA mutational analysis; Diabetes mellitus; Diabète; Megaloblastic anemia; Sensorineural hearing loss; Surdité neurosensorielle; Thiamine deficiency
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Year: 2018 PMID: 30031565 DOI: 10.1016/j.revmed.2018.06.005
Source DB: PubMed Journal: Rev Med Interne ISSN: 0248-8663 Impact factor: 0.728