Literature DB >> 29875428

The impact of variant classification on the clinical management of hereditary cancer syndromes.

Scott A Turner1, Smita K Rao2, R Hayes Morgan2, Cindy L Vnencak-Jones3, Georgia L Wiesner2,4.   

Abstract

PURPOSE: The reclassification of genetic variants poses a significant challenge for laboratories and clinicians. Variant review has resulted in the reclassification of variants of unknown significance as well as the reclassification of previously established pathogenic and likely pathogenic variants. These reclassifications have the potential to alter the clinical management of patients with hereditary cancer syndromes.
METHODS: Results were reviewed for 1694 patients seen for hereditary cancer evaluation between August 2012 and May 2017 to determine the frequency and types of variant reclassification. Patients with reclassifications with high potential for impact were monitored for alterations in organ surveillance, prophylactic surgery, and cascade testing.
RESULTS: One hundred forty-two variants were reclassified representing 124/1694 (7.3%) patients; 11.3% of reclassifications (16/142) had a high potential for clinical impact with 94% (15/16) altering clinical management of patients with 56% (9/16) changing multiple areas of management.
CONCLUSION: While reclassifications are rare, the impact on clinical management is profound. In many cases, patients with downgraded pathogenic/likely pathogenic variants had years of unnecessary organ surveillance and underwent unneeded surgical intervention. In addition, cascade testing misidentified those at risk for developing cancers, thereby altering the management across generations. The frequency and types of alterations to clinical management highlight the need for timely variant reclassification.

Entities:  

Keywords:  Clinical impact; Hereditary cancer clinic; Hereditary cancer syndrome; Variant reclassification,

Mesh:

Year:  2018        PMID: 29875428     DOI: 10.1038/s41436-018-0063-z

Source DB:  PubMed          Journal:  Genet Med        ISSN: 1098-3600            Impact factor:   8.822


  12 in total

Review 1.  Clinical application of next-generation sequencing to the practice of neurology.

Authors:  Jessica Rexach; Hane Lee; Julian A Martinez-Agosto; Andrea H Németh; Brent L Fogel
Journal:  Lancet Neurol       Date:  2019-05       Impact factor: 44.182

2.  The Responsibility to Recontact Research Participants after Reinterpretation of Genetic and Genomic Research Results.

Authors:  Yvonne Bombard; Kyle B Brothers; Sara Fitzgerald-Butt; Nanibaa' A Garrison; Leila Jamal; Cynthia A James; Gail P Jarvik; Jennifer B McCormick; Tanya N Nelson; Kelly E Ormond; Heidi L Rehm; Julie Richer; Emmanuelle Souzeau; Jason L Vassy; Jennifer K Wagner; Howard P Levy
Journal:  Am J Hum Genet       Date:  2019-04-04       Impact factor: 11.025

3.  Quantification of Discordant Variant Interpretations in a Large Family-Based Study of Li-Fraumeni Syndrome.

Authors:  Megan N Frone; Douglas R Stewart; Sharon A Savage; Payal P Khincha
Journal:  JCO Precis Oncol       Date:  2021-11-10

4.  Clinical Interpretation of Sequence Variants.

Authors:  Junyu Zhang; Yanyi Yao; Haixian He; Jun Shen
Journal:  Curr Protoc Hum Genet       Date:  2020-06

5.  Data sharing to improve concordance in variant interpretation across laboratories: results from the Canadian Open Genetics Repository.

Authors:  Chloe Mighton; Amanda C Smith; Justin Mayers; Robert Tomaszewski; Sherryl Taylor; Stacey Hume; Ron Agatep; Elizabeth Spriggs; Harriet E Feilotter; Laura Semenuk; Henry Wong; Lorena Lazo de la Vega; Christian R Marshall; Michelle M Axford; Talia Silver; George S Charames; Vanessa Di Gioacchino; Nicholas Watkins; William D Foulkes; Marcos Clavier; Nancy Hamel; George Chong; Ryan E Lamont; Jillian Parboosingh; Aly Karsan; Ian Bosdet; Sean S Young; Tracy Tucker; Mohammad Reza Akbari; Marsha D Speevak; Andrea K Vaags; Matthew S Lebo; Jordan Lerner-Ellis
Journal:  J Med Genet       Date:  2021-04-19       Impact factor: 5.941

6.  Patient perspectives on variant reclassification after cancer susceptibility testing.

Authors:  Colin M E Halverson; Laurie M Connors; Bronson C Wessinger; Ellen W Clayton; Georgia L Wiesner
Journal:  Mol Genet Genomic Med       Date:  2020-04-24       Impact factor: 2.183

7.  The effects of genomic germline variant reclassification on clinical cancer care.

Authors:  Thomas P Slavin; Sophia Manjarrez; Colin C Pritchard; Stacy Gray; Jeffrey N Weitzel
Journal:  Oncotarget       Date:  2019-01-11

Review 8.  Hereditary Predisposition to Prostate Cancer: From Genetics to Clinical Implications.

Authors:  Andreia Brandão; Paula Paulo; Manuel R Teixeira
Journal:  Int J Mol Sci       Date:  2020-07-16       Impact factor: 5.923

9.  Is 'likely pathogenic' really 90% likely? Reclassification data in ClinVar.

Authors:  Steven M Harrison; Heidi L Rehm
Journal:  Genome Med       Date:  2019-11-21       Impact factor: 11.117

10.  iVar, an Interpretation-Oriented Tool to Manage the Update and Revision of Variant Annotation and Classification.

Authors:  Sara Castellano; Federica Cestari; Giovanni Faglioni; Elena Tenedini; Marco Marino; Lucia Artuso; Rossella Manfredini; Mario Luppi; Tommaso Trenti; Enrico Tagliafico
Journal:  Genes (Basel)       Date:  2021-03-08       Impact factor: 4.096

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