| Literature DB >> 29770363 |
George K Papadimas1, George P Paraskevas1, Thomas Zambelis1, Chrisostomos Karagiaouris1, Mara Bourbouli1, Anastasia Bougea1, Maggie C Walter2, Nicolas U Schumacher2, Sabine Krause2, Elisabeth Kapaki1.
Abstract
VCP-proteinopathy is a multisystem neurodegenerative disorder caused by mutations in valosin containing protein. Here, we report the first Greek case of VCP-proteinopathy in a 62 year old patient with a slowly progressing muscular weakness since his mid-40s and a severe deterioration during the last year. He also manifested dementia with prominent neuropsychiatric symptoms, including aggression, apathy, palilalia and obsessions. Brain MRI revealed frontal atrophy, while muscle MRI showed diffuse muscle atrophy. Family history was positive and several members of the family had been diagnosed with motor neuron disease, dementia or behavioral symptoms. Sequencing of the VCP gene revealed a pathogenic heterozygous missense mutation p.R159H. Conclusively, the present report highlights the intrafamilial variability and broadens the phenotypic spectrum of VCP-proteinopathy.Entities:
Keywords: ALS; VCP; dementia
Mesh:
Substances:
Year: 2017 PMID: 29770363 PMCID: PMC5953233
Source DB: PubMed Journal: Acta Myol ISSN: 1128-2460