| Literature DB >> 29533680 |
Mehdi Zarrei1, Geoffrey G Hicks2, James N Reynolds3,4, Bhooma Thiruvahindrapuram1, Worrawat Engchuan1, Molly Pind2, Sylvia Lamoureux1, John Wei1, Zhouzhi Wang1, Christian R Marshall1, Richard F Wintle1, Albert E Chudley5,6, Stephen W Scherer1,7.
Abstract
Fetal alcohol spectrum disorder (FASD) is characterized by a combination of neurological, developmental, and congenital defects that may occur as a consequence of prenatal alcohol exposure. Earlier reports showed that large chromosomal anomalies may link to FASD. Here, we examined the prevalence and types of copy number variations (CNVs) in FASD cases previously diagnosed by a multidisciplinary FASD team in sites across Canada. We genotyped 95 children with FASD and 87 age-matched, typically developing controls on the Illumina Human Omni2.5 SNP (single nucleotide polymorphisms) array platform. We compared their CNVs with those of 10 851 population controls to identify rare CNVs (<0.1% frequency), which may include large unbalanced chromosomal abnormalities, that might be relevant to FASD. In 12/95 (13%) of the FASD cases, rare CNVs were found that impact potentially clinically relevant developmental genes, including the CACNA1H involved in epilepsy and autism, the 3q29 deletion disorder, and others. Our results show that a subset of children diagnosed with FASD have chromosomal deletions and duplications that may co-occur or explain the neurodevelopmental impairments in a diagnosed cohort of FASD individuals. Children suspected to have FASD with or without sentinel facial features of fetal alcohol syndrome and neurodevelopmental delays should potentially be evaluated by a clinical geneticist and possibly have genetic investigations as appropriate to exclude other etiologies.Entities:
Keywords: CNV; FASD; TSAF; copy number variations; fetal alcohol spectrum disorder; troubles du spectre de l’alcoolisation fœtale; variabilité du nombre de copies
Mesh:
Year: 2018 PMID: 29533680 DOI: 10.1139/bcb-2017-0241
Source DB: PubMed Journal: Biochem Cell Biol ISSN: 0829-8211 Impact factor: 3.626