Literature DB >> 29476300

Homozygous nonsense mutation Trp28X in the LHB gene causes male hypogonadism.

Xiaoyu Yang1, H Ochin1, Li Shu1, Jinyong Liu1, Jiandong Shen1, Jiayin Liu1, Changsong Lin2, Yugui Cui3.   

Abstract

PURPOSE: The purpose of this study was to investigate a novel mutation in the luteinizing hormone beta-subunit (LHB) gene in one male patient with hypogonadism due to selective luteinizing hormone (LH) deficiency.
METHODS: Sanger sequencing of one 28-year-old man born to consanguineous parents was performed. Treatment with human chorionic gonadotropin (hCG) (2000 IU, twice a week) was initiated for 3 months, followed by 5000 IU weekly to date.
RESULTS: We identified a novel c.84G>A[p.W28X] nonsense LHB mutation. The W28X mutation produces a truncated LHB peptide of seven amino acids, which prevents the synthesis of intact LH. After 40 days of treatment with hCG, the patient exhibited a few spermatozoa in the semen. Treated for 6 months, the patient exhibited normal seminal parameters.
CONCLUSIONS: We identified a novel mutation in the LHB gene in a male patient with hypogonadism and provided evidence that LHB nonsense mutation can cause selective LH deficiency. We reconfirmed hCG treatment may restore male fertility due to LHB mutation.

Entities:  

Keywords:  Luteinizing hormone; Luteinizing hormone beta subunit; Primary hypogonadotropic hypogonadism; Selective luteinizing hormone deficiency

Mesh:

Substances:

Year:  2018        PMID: 29476300      PMCID: PMC5984881          DOI: 10.1007/s10815-018-1133-5

Source DB:  PubMed          Journal:  J Assist Reprod Genet        ISSN: 1058-0468            Impact factor:   3.412


  20 in total

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