| Literature DB >> 29383495 |
Jun Nakamura1,2, Takuto Hikichi3, Haruhiro Inoue4, Ko Watanabe1,2, Hitomi Kikuchi1,2, Tadayuki Takagi2, Rei Suzuki2, Mitsuru Sugimoto2, Naoki Konno2, Yuichi Waragai2, Hiroyuki Asama2, Mika Takasumi2, Yuki Sato2, Hiroki Irie2, Katsutoshi Obara5, Hiromasa Ohira2.
Abstract
Allgrove syndrome, also known as Triple A syndrome, is a rare autosomal recessive genetic disease characterized by three signs: esophageal achalasia, adrenocorticotropic hormone refractoriness, and alacrima. A 31-year-old male presented to our hospital for treatment of difficulty swallowing caused by esophageal achalasia. Because he had complicating alacrima, a neurologic disease, and a family history of consanguineous marriage, a genetic neurologic disease was suspected. Then, a mutation in the achalasia-addisonianism-alacrima syndrome gene was identified. With the diagnosis of Allgrove syndrome, a per-oral endoscopic myotomy (POEM) was performed for esophageal achalasia. After the POEM, the symptoms and the esophageal pressure findings ameliorated quickly, with no recurrence noted throughout a follow-up of more than 1 year. Here, we report the first case of POEM performed for esophageal achalasia in Allgrove syndrome.Entities:
Keywords: Alacrima; Allgrove syndrome; Dysphagia; Esophageal achalasia; Per-oral endoscopic myotomy
Mesh:
Year: 2018 PMID: 29383495 DOI: 10.1007/s12328-018-0819-7
Source DB: PubMed Journal: Clin J Gastroenterol ISSN: 1865-7265