Literature DB >> 29299872

Coping Strategies, Stress, and Support Needs in Caregivers of Children with Mucopolysaccharidosis.

Amy Schadewald1, Ericka Kimball2, Li Ou3.   

Abstract

The mucopolysaccharidoses are a set of rare, inherited conditions that can have a catastrophic impact on those affected and their families. Because of the rarity of these disorders, little is known regarding the challenges faced by families of those affected and what coping mechanisms are commonly used. Coping is a way to manage demands that occur in one's environment or within oneself. Medical social workers historically have facilitated this process while providing support to patients who are responding to pressures of their diagnosis and the system.A questionnaire of demographics and qualitative questions, along with the Pediatric Inventory for Parents (PIP) and Brief COPE, was sent by electronic survey to caregivers of children with MPS. The results of Brief COPE showed that problem-focused coping was more frequently used than emotion-focused (p < 0.001) or dysfunctional coping (p < 0.0001). Acceptance was the most frequently used coping strategy (p < 0.05). The results of PIP showed that emotionally distressing events were the most difficult (p < 0.001), while events related to medical care occurred at the highest frequency (p < 0.001). Psychosocial support provided by medical social workers significantly increased acceptance of caregivers (p = 0.04). Guidance on what to expect provided by any member of the care team increased denial (p = 0.02) and the difficulty of emotional distress (p = 0.04). This study identified commonly used coping strategies and measured stress among caregivers of children with MPS, as well as access to and use of psychosocial support services. Results highlight the urgency to improve the coverage and quality of psychosocial support and other support services.

Entities:  

Keywords:  Coping; Mucopolysaccharidosis; Parental stress; Psychosocial support; Questionnaire; Rare disease

Year:  2018        PMID: 29299872      PMCID: PMC6226403          DOI: 10.1007/8904_2017_87

Source DB:  PubMed          Journal:  JIMD Rep        ISSN: 2192-8304


  15 in total

1.  Validity and reliability of the brief COPE in carers of people with dementia: the LASER-AD Study.

Authors:  Claudia Cooper; Cornelius Katona; Gill Livingston
Journal:  J Nerv Ment Dis       Date:  2008-11       Impact factor: 2.254

2.  Reliability and validity of the Brief COPE Scale (English version) among women with breast cancer undergoing treatment of adjuvant chemotherapy: a Malaysian study.

Authors:  N Yusoff; W Y Low; C H Yip
Journal:  Med J Malaysia       Date:  2010-03

3.  You want to measure coping but your protocol's too long: consider the brief COPE.

Authors:  C S Carver
Journal:  Int J Behav Med       Date:  1997

4.  Behaviour in mucopolysaccharide disorders.

Authors:  M C Bax; G A Colville
Journal:  Arch Dis Child       Date:  1995-07       Impact factor: 3.791

Review 5.  Coping theory and research: past, present, and future.

Authors:  R S Lazarus
Journal:  Psychosom Med       Date:  1993 May-Jun       Impact factor: 4.312

6.  Childhood illness-related parenting stress: the pediatric inventory for parents.

Authors:  R Streisand; S Braniecki; K P Tercyak; A E Kazak
Journal:  J Pediatr Psychol       Date:  2001 Apr-May

7.  Thinking big, supporting families and enabling coping: the value of social work in patient and family centered health care.

Authors:  Shelley L Craig; Itanni Betancourt; Barbara Muskat
Journal:  Soc Work Health Care       Date:  2015

8.  Parental social support, coping strategies, resilience factors, stress, anxiety and depression levels in parents of children with MPS III (Sanfilippo syndrome) or children with intellectual disabilities (ID).

Authors:  Sheena Grant; Elaine Cross; James Edmond Wraith; Simon Jones; Louise Mahon; Michelle Lomax; Brian Bigger; Dougal Hare
Journal:  J Inherit Metab Dis       Date:  2012-11-15       Impact factor: 4.982

9.  Developmental and degenerative patterns associated with cognitive, behavioural and motor difficulties in the Sanfilippo syndrome: an epidemiological study.

Authors:  F D Nidiffer; T E Kelly
Journal:  J Ment Defic Res       Date:  1983-09

10.  Phenotype prediction for mucopolysaccharidosis type I by in silico analysis.

Authors:  Li Ou; Michael J Przybilla; Chester B Whitley
Journal:  Orphanet J Rare Dis       Date:  2017-07-04       Impact factor: 4.123

View more
  6 in total

Review 1.  Unmet Cardiac Clinical Needs in Adult Mucopolysaccharidoses.

Authors:  Karolina M Stepien; Elizabeth A Braunlin
Journal:  Front Cardiovasc Med       Date:  2022-06-10

2.  Rare disease awareness and perspectives of physicians in China: a questionnaire-based study.

Authors:  Xuefeng Li; Xiangyu Zhang; Shu Zhang; Zijuan Lu; Jianyong Zhang; Jincheng Zhou; Bingzhe Li; Li Ou
Journal:  Orphanet J Rare Dis       Date:  2021-04-13       Impact factor: 4.123

Review 3.  A systematic review and integrative sequential explanatory narrative synthesis: The psychosocial impact of parenting a child with a lysosomal storage disorder.

Authors:  Sadie Hassall; Debbie Michelle Smith; Stewart Rust; Anja Wittkowski
Journal:  J Inherit Metab Dis       Date:  2022-02-24       Impact factor: 4.750

4.  Iranian future healthcare professionals' knowledge and opinions about rare diseases: cross-sectional study.

Authors:  Reza Jahanshahi; Amirreza Nasirzadeh; Mahan Farzan; Jan Domaradzki; Leila Jouybari; Akram Sanagoo; Mahour Farzan; Komeil Aghazadeh-Habashi; Ahmadreza Fallah Faraghe; Sadegh Bagheri; Marziyeh Samiee; Arina Ansari; Kimia Eskandari; Negar Namakkoobi; Fatemeh Soltanimoghadam; Hadi Mashali; Erfan Yavari; Saba Bay; Nafiseh Memaripanah; Elahe Meftah; Saeed Amanzadeh; Fatemeh Talati; Sasan Bahramzadeh
Journal:  Orphanet J Rare Dis       Date:  2022-09-29       Impact factor: 4.303

5.  A questionnaire-based study to comprehensively assess the status quo of rare disease patients and care-givers in China.

Authors:  Xuefeng Li; Meiling Liu; Jinduan Lin; Bingzhe Li; Xiangyu Zhang; Shu Zhang; Zijuan Lu; Jianyong Zhang; Jincheng Zhou; Li Ou
Journal:  Orphanet J Rare Dis       Date:  2021-07-22       Impact factor: 4.123

6.  The urgent need to empower rare disease organizations in China: an interview-based study.

Authors:  Xuefeng Li; Zijuan Lu; Jianyong Zhang; Xiangyu Zhang; Shu Zhang; Jincheng Zhou; Bingzhe Li; Li Ou
Journal:  Orphanet J Rare Dis       Date:  2020-10-12       Impact factor: 4.123

  6 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.