Literature DB >> 29276444

Widespread Vasculopathy in a Patient with Morquio A Syndrome.

Adam W Powell, Michael D Taylor, T Andrew Burrow, Robert J Hopkin, Carlos E Prada, John L Jefferies.   

Abstract

Morquio A syndrome (mucopolysaccharidosis IV type A), an autosomal recessive lysosomal storage disorder caused by a defective N-acetylgalactosamine 6-sulfatase gene, leads to lysosomal accumulation of keratan sulfate and chondroitin 6-sulfate. This accumulation affects multiple systems and causes notable cardiovascular manifestations, such as thickening of the left-sided valves, ventricular hypertrophy, and intimal stenosis of the coronary arteries. There have been few reports of vasculopathy in this population. We present the case of a 58-year-old woman with Morquio A syndrome who was found to have aortic dilation on a routine screening echocardiogram. Magnetic resonance images revealed multiple tortuous, dilated arteries in her head, neck, and abdomen. The diffuse vasculopathy seen in this patient should prompt further study to determine whether this is an underreported phenomenon of clinical significance or an unusual finding in this rare disorder.

Entities:  

Keywords:  Adult; aorta/pathology; cardiovascular abnormalities; heart valves/pathology; mucopolysaccharidosis IV/complications/diagnosis/diagnostic imaging/pathology

Mesh:

Year:  2017        PMID: 29276444      PMCID: PMC5737156          DOI: 10.14503/THIJ-16-6121

Source DB:  PubMed          Journal:  Tex Heart Inst J        ISSN: 0730-2347


  10 in total

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3.  Obstructive airway in Morquio A syndrome, the past, the present and the future.

Authors:  Shunji Tomatsu; Lauren W Averill; Kazuki Sawamoto; William G Mackenzie; Michael B Bober; Christian Pizarro; Christopher J Goff; Li Xie; Tadao Orii; Mary Theroux
Journal:  Mol Genet Metab       Date:  2015-09-21       Impact factor: 4.797

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Journal:  Br Heart J       Date:  1981-07

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Authors:  Christine Lavery; Chris Hendriksz
Journal:  JIMD Rep       Date:  2014-04-10

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Authors:  Marja W Wessels; Coriene E Catsman-Berrevoets; Grazia M S Mancini; Martijn H Breuning; Jeanette J M Hoogeboom; Hans Stroink; Ingrid Frohn-Mulder; Paul J Coucke; Anne De Paepe; Martinus F Niermeijer; Patrick J Willems
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8.  Pathogenesis of Morquio A syndrome: an autopsied case reveals systemic storage disorder.

Authors:  Eriko Yasuda; Kazunari Fushimi; Yasuyuki Suzuki; Katsuji Shimizu; Tsuyoshi Takami; Jozef Zustin; Pravin Patel; Kristen Ruhnke; Tsutomu Shimada; Bobbie Boyce; Terry Kokas; Carol Barone; Mary Theroux; William Mackenzie; Barbara Nagel; Jan S Ryerse; Kenji E Orii; Hiroki Iida; Tadao Orii; Shunji Tomatsu
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Authors:  Christian J Hendriksz; Kenneth I Berger; Roberto Giugliani; Paul Harmatz; Christoph Kampmann; William G Mackenzie; Julian Raiman; Martha Solano Villarreal; Ravi Savarirayan
Journal:  Am J Med Genet A       Date:  2014-10-24       Impact factor: 2.802

10.  Heart and Cardiovascular Involvement in Patients with Mucopolysaccharidosis Type IVA (Morquio-A Syndrome).

Authors:  Christoph Kampmann; Tariq Abu-Tair; Seyfullah Gökce; Christina Lampe; Jörg Reinke; Eugen Mengel; Julia B Hennermann; Christiane M Wiethoff
Journal:  PLoS One       Date:  2016-09-09       Impact factor: 3.240

  10 in total

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