Literature DB >> 29230162

A Novel de novo FZD2 Mutation in a Patient with Autosomal Dominant Omodysplasia.

Seval Türkmen1,2, Malte Spielmann1,3, Nilay Güneş4, Alexej Knaus1,3,5, Ricarda Flöttmann1, Stefan Mundlos1,3, Beyhan Tüysüz4.   

Abstract

We described a heterozygous de novo mutation (G434V) in the frizzled class receptor 2 (FZD2) gene in a patient with distinct facial features including hypertelorism, bilateral cleft lip/palate, short nose with a broad nasal bridge, microretrognathia, and bilateral shortness of the upper limbs, first metacarpal bones, and middle phalanges of the 5th digits. The findings of our patient were compared to an autosomal dominant omodysplasia (OMOD2) family with FZD2 mutation reported in the literature. OMOD2 is a rare skeletal dysplasia and characterized by facial dysmorphism and shortness of the upper extremities and first metacarpal bones. This is the second report which supports the findings of the first family described and points out that heterozygous FZD2 mutations may be disease-causing for OMOD2.

Entities:  

Keywords:  FZD2; Frizzled-2; OMOD2; Omodysplasia

Year:  2017        PMID: 29230162      PMCID: PMC5701278          DOI: 10.1159/000479721

Source DB:  PubMed          Journal:  Mol Syndromol        ISSN: 1661-8769


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4.  Two unrelated patients with autosomal dominant omodysplasia and FRIZZLED2 mutations.

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