| Literature DB >> 29088509 |
Maria F Bedeschi1, Sara Giangiobbe1, Leda Paganini2, Silvia Tabano2, Rosamaria Silipigni3, Lorenzo Colombo4, Beatrice L Crippa4, Faustina Lalatta1, Silvana Guerneri3, Monica Miozzo2.
Abstract
The STAR syndrome is a rare X-linked dominant developmental disorder caused by point mutations in the single FAM58A gene or deletions involving FAM58A and its flanking genes. The STAR phenotype is characterized by a rather homogeneous constellation of facial dysmorphisms and malformations summarized by its acronym, Syndactyly, Telecanthus, Anogenital, and Renal malformations. Here we describe a female patient with STAR syndrome and a 130 kb deletion at Xq28, including the FAM58A gene. She presented with cleft lip palate, omphalocele, and cerebral malformations not previously considered part of the phenotypic spectrum of this syndrome. She died at 6 weeks from respiratory failure.Entities:
Keywords: FAM58A; STAR syndrome
Mesh:
Substances:
Year: 2017 PMID: 29088509 DOI: 10.1002/ajmg.a.38484
Source DB: PubMed Journal: Am J Med Genet A ISSN: 1552-4825 Impact factor: 2.802