Literature DB >> 29031008

Identification of a novel homozygous TRAPPC9 gene mutation causing non-syndromic intellectual disability, speech disorder, and secondary microcephaly.

Ansar A Abbasi1, Kathrin Blaesius2,3,4, Hao Hu5, Zahid Latif6, Sylvie Picker-Minh2,3,4,7, Muhammad N Khan6, Sundas Farooq1, Muzammil A Khan8, Angela M Kaindl2,3,4,7.   

Abstract

TRAPPC9 gene mutations have been linked recently to autosomal recessive mental retardation 13 (MRT13; MIM#613192) with only eight families reported world-wide. We assessed patients from two consanguineous pedigrees of Pakistani descent with non-syndromic intellectual disability and postnatal microcephaly through whole exome sequencing (WES) and cosegregation analysis. Here we report six further patients from two pedigrees with homozygous TRAPPC9 gene mutations, the novel nonsense mutation c.2065G>T (p.E689*) and the previously identified nonsense mutation c.1423C>T (p.R475*). We provide an overview of previously reported clinical features and highlight common symptoms and variability of MRT13. Common findings are intellectual disability and absent speech, and frequently microcephaly, motor delay and pathological findings on MRI including diminished cerebral white matter volume are present. Mutations in TRAPPC9 should be considered in non-syndromic autosomal recessive intellectual disability with severe speech disorder.
© 2017 Wiley Periodicals, Inc.

Entities:  

Keywords:  NF-κB signaling; TRAPPC9 gene; autosomal recessive intellectual disability; microcephaly; vesicle trafficking

Mesh:

Substances:

Year:  2017        PMID: 29031008     DOI: 10.1002/ajmg.b.32602

Source DB:  PubMed          Journal:  Am J Med Genet B Neuropsychiatr Genet        ISSN: 1552-4841            Impact factor:   3.568


  11 in total

1.  Distinct Autism Spectrum Disorder Phenotype and Hand-Flapping Stereotypes: Two Siblings with Novel Homozygous Mutation in TRAPPC9 Gene and Literature Review.

Authors:  Hilmi Bolat; Gül Ünsel-Bolat; Hatice Derin; Aşkın Şen; Serdar Ceylaner
Journal:  Mol Syndromol       Date:  2022-03-09

2.  Trappc9 deficiency in mice impairs learning and memory by causing imbalance of dopamine D1 and D2 neurons.

Authors:  Yuting Ke; Meiqian Weng; Gaurav Chhetri; Muhammad Usman; Yan Li; Qing Yu; Yingzhuo Ding; Zejian Wang; Xiaolong Wang; Pinky Sultana; Marian DiFiglia; Xueyi Li
Journal:  Sci Adv       Date:  2020-11-18       Impact factor: 14.136

3.  Novel Compound Heterozygous Mutations in the TRAPPC9 Gene in Two Siblings With Autism and Intellectual Disability.

Authors:  Areerat Hnoonual; Potchanapond Graidist; Supika Kritsaneepaiboon; Pornprot Limprasert
Journal:  Front Genet       Date:  2019-02-11       Impact factor: 4.599

4.  Profound intellectual disability caused by homozygous TRAPPC9 pathogenic variant in a man from Malta.

Authors:  Katelynn M Wilton; Lauren B Gunderson; Linda Hasadsri; Christopher P Wood; Lisa A Schimmenti
Journal:  Mol Genet Genomic Med       Date:  2020-03-11       Impact factor: 2.183

Review 5.  ER-to-Golgi Trafficking and Its Implication in Neurological Diseases.

Authors:  Bo Wang; Katherine R Stanford; Mondira Kundu
Journal:  Cells       Date:  2020-02-11       Impact factor: 6.600

6.  Two Novel Compound Heterozygous Mutations in the TRAPPC9 Gene Reveal a Connection of Non-syndromic Intellectual Disability and Autism Spectrum Disorder.

Authors:  Johannes Krämer; Meinrad Beer; Harald Bode; Benedikt Winter
Journal:  Front Genet       Date:  2021-02-25       Impact factor: 4.599

Review 7.  Emerging role of NIK/IKK2-binding protein (NIBP)/trafficking protein particle complex 9 (TRAPPC9) in nervous system diseases.

Authors:  Brittany Bodnar; Arianna DeGruttola; Yuanjun Zhu; Yuan Lin; Yonggang Zhang; Xianming Mo; Wenhui Hu
Journal:  Transl Res       Date:  2020-05-17       Impact factor: 7.012

8.  A Single-Step Genome Wide Association Study on Body Size Traits Using Imputation-Based Whole-Genome Sequence Data in Yorkshire Pigs.

Authors:  Huatao Liu; Hailiang Song; Yifan Jiang; Yao Jiang; Fengxia Zhang; Yibing Liu; Yong Shi; Xiangdong Ding; Chuduan Wang
Journal:  Front Genet       Date:  2021-07-02       Impact factor: 4.599

9.  Discrimination of DNA Methylation Signal from Background Variation for Clinical Diagnostics.

Authors:  Robersy Sanchez; Xiaodong Yang; Thomas Maher; Sally A Mackenzie
Journal:  Int J Mol Sci       Date:  2019-10-27       Impact factor: 5.923

10.  Identification of two novel homozygous nonsense mutations in TRAPPC9 in two unrelated consanguineous families with intellectual Disability from Iran.

Authors:  Farideh Yousefipour; Hossein Mozhdehipanah; Frouzandeh Mahjoubi
Journal:  Mol Genet Genomic Med       Date:  2021-01-29       Impact factor: 2.183

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