Literature DB >> 29027576

Neonatal ulcerative colitis associated with Familial Mediterranean fever: a case report.

Elif Sag1, Ferhat Demir2, Mustafa Emre Ercin3, Mukaddes Kalyoncu2, Murat Cakir4.   

Abstract

Neonatal inflammatory bowel disease (IBD) is a subclass of very early onset IBD that includes children younger than 1 month. It is characterized by more colonic involvement and monogenetic etiology, resistance to classical anti-inflammatory/immunomodulatory treatments and associated with colitis in first-degree family members. Herein we report a 3 month-old girl who was admitted with bloody diarrhea since 10 days of age. Her symptoms persist despite diet elimination. She was diagnosed with neonatal ulcerative colitis (UC) based on clinical, laboratory and histopathological examination. But, she was unresponsive to the immunosuppressive therapy. On the follow-up, she was hospitalized for the high fever two times. Genetic analysis revealed homozygote M694 V mutation. Bloody diarrhea and other clinical findings were improved after colchicine therapy. Neonatal UC associated with Familial Mediterranean fever is an extremely rare condition and to the best of our knowledge our case is the first case in literature. Early diagnosis autoinflammatory disease may prevent complications related to unnecessary immunosuppressive drug usage and the risk of development of amyloidosis associated with autoinflammatory disorders.

Entities:  

Keywords:  Familial Mediterranean fever; Neonatal; Ulcerative colitis

Mesh:

Substances:

Year:  2017        PMID: 29027576     DOI: 10.1007/s00296-017-3848-5

Source DB:  PubMed          Journal:  Rheumatol Int        ISSN: 0172-8172            Impact factor:   2.631


  17 in total

Review 1.  Familial Mediterranean fever, review of the literature.

Authors:  Mansour Alghamdi
Journal:  Clin Rheumatol       Date:  2017-06-18       Impact factor: 2.980

2.  Association of inflammatory bowel disease with familial Mediterranean fever in Turkish children.

Authors:  Omer F Beşer; Ozgür Kasapçopur; Fügen Cullu Cokuğraş; Tufan Kutlu; Nil Arsoy; Tülay Erkan
Journal:  J Pediatr Gastroenterol Nutr       Date:  2013-05       Impact factor: 2.839

3.  Detection of Mediterranean fever gene mutations in Egyptian children with inflammatory bowel disease.

Authors:  Samia Salah; Mortada El-Shabrawi; Hala Mohamed Lotfy; Hala Fathy Shiba; Maha Abou-Zekri; Yomna Farag
Journal:  Int J Rheum Dis       Date:  2014-10-08       Impact factor: 2.454

4.  The association of inflammatory bowel disease and Mediterranean fever gene (MEFV) mutations in Turkish children.

Authors:  Nuray Uslu; Aysel Yüce; Hülya Demir; Inci N Saltik-Temizel; Yusuf Usta; Engin Yilmaz; Nesrin Beşbaş; Figen Gürakan; Hasan Ozen; Seza Ozen
Journal:  Dig Dis Sci       Date:  2010-03-21       Impact factor: 3.199

5.  Children with early-onset inflammatory bowel disease (IBD): analysis of a pediatric IBD consortium registry.

Authors:  Melvin B Heyman; Barbara S Kirschner; Benjamin D Gold; George Ferry; Robert Baldassano; Stanley A Cohen; Harland S Winter; Patricia Fain; Chris King; Terry Smith; Hashem B El-Serag
Journal:  J Pediatr       Date:  2005-01       Impact factor: 4.406

6.  Epidemiologic and clinical characteristics of children with newly diagnosed inflammatory bowel disease in Wisconsin: a statewide population-based study.

Authors:  Subra Kugathasan; Robert H Judd; Raymond G Hoffmann; Janice Heikenen; Gregorz Telega; Farhat Khan; Sally Weisdorf-Schindele; William San Pablo; Jean Perrault; Roger Park; Michael Yaffe; Christopher Brown; Maria T Rivera-Bennett; Issam Halabi; Alfonso Martinez; Ellen Blank; Steven L Werlin; Colin D Rudolph; David G Binion
Journal:  J Pediatr       Date:  2003-10       Impact factor: 4.406

7.  An infant with severe refractory Crohn's disease and homozygous MEFV mutation who dramatically responded to colchicine.

Authors:  Zarife Kuloğlu; Aydan Kansu; Gonca Ustündağ; Z Birsin Özçakar; Arzu Ensari; Mesiha Ekim
Journal:  Rheumatol Int       Date:  2010-01-05       Impact factor: 2.631

8.  The familial Mediterranean fever (MEFV) gene may be a modifier factor of inflammatory bowel disease in infancy.

Authors:  Sinan Sari; Odul Egritas; Buket Dalgic
Journal:  Eur J Pediatr       Date:  2007-05-23       Impact factor: 3.183

9.  Pediatric modification of the Montreal classification for inflammatory bowel disease: the Paris classification.

Authors:  Arie Levine; Anne Griffiths; James Markowitz; David C Wilson; Dan Turner; Richard K Russell; John Fell; Frank M Ruemmele; Thomas Walters; Mary Sherlock; Marla Dubinsky; Jeffrey S Hyams
Journal:  Inflamm Bowel Dis       Date:  2010-11-08       Impact factor: 5.325

Review 10.  The diagnostic approach to monogenic very early onset inflammatory bowel disease.

Authors:  Holm H Uhlig; Tobias Schwerd; Sibylle Koletzko; Neil Shah; Jochen Kammermeier; Abdul Elkadri; Jodie Ouahed; David C Wilson; Simon P Travis; Dan Turner; Christoph Klein; Scott B Snapper; Aleixo M Muise
Journal:  Gastroenterology       Date:  2014-07-21       Impact factor: 33.883

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  1 in total

1.  Evaluation of the Clinical Effects and Frequency of MEFV Gene Mutation in Patients with Inflammatory Bowel Disease.

Authors:  S Sahin; D Gulec; S Günay; C Cekic
Journal:  Gastroenterol Res Pract       Date:  2021-11-15       Impact factor: 2.260

  1 in total

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