Literature DB >> 28970704

Hemophagocytic Lymphohistiocytosis Masquerading as Acute Liver Failure: A Single Center Experience.

Nitin Jagtap1, Mithun Sharma1, Gupta Rajesh1, Padaki Nagaraja Rao1, Sekaran Anuradha1, Manu Tandan1, Mohan Ramchandani1, Duvvuru Nageshwar Reddy1.   

Abstract

BACKGROUND/AIM: Hemophagocytic lymphohistiocytosis (HLH) is a potentially life-threatening disorder of extreme inflammation and unregulated immune response which require prompt recognition and early introduction of definitive therapy. HLH can present with wide range of hepatic dysfunction ranging from mild elevation of transaminases to liver failure. This study is carried out to describe the clinical and laboratory presentation of HLH.
METHODS: Patients who were diagnosed with HLH between January 2013 and December 2015 were retrospectively included in this study.
RESULTS: Six patients were diagnosed as secondary HLH with median age of 28.5 years at diagnosis. All patients were presented with history of deep jaundice and high grade fever with pancytopenia and splenomegaly. Underlying diagnosis was viral infections in 4 and probable viral infection in remaining two. Bone marrow hemophagocytosis was present in 3 cases. Three patients were treated with corticosteroids only and one each with corticosteroids with cyclosporine or intravenous immunoglobulin (IVIG) and HLH treatment protocol. One patient died due to acute respiratory distress syndrome (ARDS); another patient died in follow-up due to respiratory failure due to pneumonia.
CONCLUSIONS: HLH is rare and potentially life-threatening cause of prolonged fever, jaundice and pancytopenia. Early diagnosis and initiation of specific therapy can improve clinical outcome.

Entities:  

Keywords:  ARDS, acute respiratory distress syndrome; CMV, cytomegalovirus; CSA, cyclosporine; EBV, Epstein Barr virus; HLH, hemophagocytic lymphohistiocytosis; IVIG, intravenous immunoglobulin; MAS, macrophage activation syndrome; acute liver failure; hepatotoxicity; viral hepatitis

Year:  2017        PMID: 28970704      PMCID: PMC5620357          DOI: 10.1016/j.jceh.2017.01.119

Source DB:  PubMed          Journal:  J Clin Exp Hepatol        ISSN: 0973-6883


  26 in total

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Authors:  Jan-Inge Henter; Annacarin Horne; Maurizio Aricó; R Maarten Egeler; Alexandra H Filipovich; Shinsaku Imashuku; Stephan Ladisch; Ken McClain; David Webb; Jacek Winiarski; Gritta Janka
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9.  Haemophagocytic lymphohistiocytosis in adults: a multicentre case series over 7 years.

Authors:  Alison M Schram; Paige Comstock; Meghan Campo; Daniel Gorovets; Ann Mullally; Kelly Bodio; Jon Arnason; Nancy Berliner
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10.  Highly elevated ferritin levels and the diagnosis of hemophagocytic lymphohistiocytosis.

Authors:  Carl E Allen; Xiaoying Yu; Claudia A Kozinetz; Kenneth L McClain
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1.  Acute liver failure secondary to severe systemic disease from fatal hemophagocytic lymphohistiocytosis: Case report and systematic literature review.

Authors:  Mitchell S Cappell; Ismail Hader; Mitual Amin
Journal:  World J Hepatol       Date:  2018-09-27

2.  Clinical characteristics of liver failure with hemophagocytic lymphohistiocytosis.

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Journal:  Sci Rep       Date:  2019-05-31       Impact factor: 4.379

Review 3.  Macrophage Activation-Like Syndrome: A Distinct Entity Leading to Early Death in Sepsis.

Authors:  Eleni Karakike; Evangelos J Giamarellos-Bourboulis
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4.  A novel prognostic model for adult patients with Hemophagocytic Lymphohistiocytosis.

Authors:  Jun Zhou; Jing Zhou; Zhi-Qi Wu; Hemant Goyal; Hua-Guo Xu
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  4 in total

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