Literature DB >> 28914566

A novel ETFDH mutation in an adult patient with late-onset riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency.

Min Chen1, Jing Peng1, Wei Wei1, Rui Wang1, Hongliang Xu1, Hongbo Liu1.   

Abstract

AIM OF THE STUDY: To report a novel mutation in the electron transfer flavoprotein dehydrogenase (ETFDH) gene in an adult patient with late-onset riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency.
MATERIALS AND METHODS: The genomic DNAs from a patient whose main clinical presentations are muscles weakness and hypoglycemia was analysed.
RESULTS: The patient was identified to carry compound heterozygous mutations in ETFDH gene. Two missense mutations c.814 G > A and c.389 A > T were found.
CONCLUSION: This is the first report of c.814G > A mutation in ETFDH in adult patient with MADD.

Entities:  

Keywords:  ETFDH; MADD; mutation; novel

Mesh:

Substances:

Year:  2017        PMID: 28914566     DOI: 10.1080/00207454.2017.1380641

Source DB:  PubMed          Journal:  Int J Neurosci        ISSN: 0020-7454            Impact factor:   2.292


  3 in total

1.  Diagnosis, genetic characterization and clinical follow up of mitochondrial fatty acid oxidation disorders in the new era of expanded newborn screening: A single centre experience.

Authors:  A Maguolo; G Rodella; A Dianin; R Nurti; I Monge; E Rigotti; G Cantalupo; L Salviati; S Tucci; F Pellegrini; G Molinaro; F Lupi; P Tonin; A Pasini; N Campostrini; F Ion Popa; F Teofoli; M Vincenzi; M Camilot; G Piacentini; A Bordugo
Journal:  Mol Genet Metab Rep       Date:  2020-08-05

2.  Clinical Features of Multiple Acyl-CoA Dehydrogenase Deficiency With ETFDH Variants in the First Korean Cases.

Authors:  Yoo Jinie Kim; Jung Min Ko; Junghan Song; Kyung A Lee
Journal:  Ann Lab Med       Date:  2018-11       Impact factor: 3.464

3.  Late-onset riboflavin-responsive multiple acyl-CoA dehydrogenase deficiency (MADD): case reports and epidemiology of ETFDH gene mutations.

Authors:  Wei Chen; Youqiao Zhang; Yifeng Ni; Shaoyu Cai; Xin Zheng; Frank L Mastaglia; Jingshan Wu
Journal:  BMC Neurol       Date:  2019-12-18       Impact factor: 2.474

  3 in total

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