Nicolas Degand1,2, Justine Dautremer3, Benoît Pilmis4, Agnès Ferroni5, Fanny Lanternier3, Julie Bruneau4, Olivier Hermine6, Stéphane Blanche7, Xavier Nassif5, Olivier Lortholary3, Marc Lecuit3. 1. Université Paris Descartes - Sorbonne Paris Cité, Laboratoire de Microbiologie, Hôpital Necker-Enfants Malades, Assistance Publique - Hôpitaux de Paris, Paris, France. degand.n@chu-nice.fr. 2. CHU de Nice, Laboratoire de Bactériologie, 151 route St Antoine de Ginestière, BP 3079, 06202, Nice, Cedex 3, France. degand.n@chu-nice.fr. 3. Université Paris Descartes - Sorbonne Paris Cité, Service de Maladies infectieuses et Tropicales, Hôpital Necker-Enfants Malades, Centre d'Infectiologie Necker-Pasteur, Assistance Publique - Hôpitaux de Paris, Paris, France. 4. Université Paris Descartes - Sorbonne Paris Cité, Service d'Anatomopathologie, Hôpital Necker-Enfants Malades, Assistance Publique - Hôpitaux de Paris, Paris, France. 5. Université Paris Descartes - Sorbonne Paris Cité, Laboratoire de Microbiologie, Hôpital Necker-Enfants Malades, Assistance Publique - Hôpitaux de Paris, Paris, France. 6. Université Paris Descartes - Sorbonne Paris Cité, Service d'Hématologie, Hôpital Necker-Enfants Malades, Assistance Publique - Hôpitaux de Paris, Paris, France. 7. Université Paris Descartes - Sorbonne Paris Cité, Service d'Immuno-hématologie pédiatrique, Hôpital Necker-Enfants Malades, Assistance Publique - Hôpitaux de Paris, Paris, France.
Abstract
ᅟ: Helicobacter bilis is a commensal bacterium causing chronic hepatitis and colitis in mice. In humans, enterohepatic Helicobacter spp. are associated with chronic hepatobiliary diseases. PURPOSE: We aimed at understanding the microbial etiology in a patient with X-linked agammaglobulinemia presenting with suppurative cholangitis. METHODS: 16S rDNA PCR directly performed on a liver biopsy retrieved DNA of H. bilis. RESULTS: Clinical outcome resulted in the normalization of clinical and biological parameters under antibiotic treatment by a combination of ceftriaxone, metronidazole, and doxycyclin followed by a 2-week treatment with moxifloxacin and a 2-month treatment with azithromycin. CONCLUSION: In conclusion, these data suggest a specific clinical and microbiological approach in patients with humoral deficiency in order to detect H. bilis hepatobiliary diseases.
ᅟ: Helicobacter bilis is a commensal bacterium causing chronic hepatitis and colitis in mice. In humans, enterohepatic Helicobacter spp. are associated with chronic hepatobiliary diseases. PURPOSE: We aimed at understanding the microbial etiology in a patient with X-linked agammaglobulinemia presenting with suppurative cholangitis. METHODS: 16S rDNA PCR directly performed on a liver biopsy retrieved DNA of H. bilis. RESULTS: Clinical outcome resulted in the normalization of clinical and biological parameters under antibiotic treatment by a combination of ceftriaxone, metronidazole, and doxycyclin followed by a 2-week treatment with moxifloxacin and a 2-month treatment with azithromycin. CONCLUSION: In conclusion, these data suggest a specific clinical and microbiological approach in patients with humoral deficiency in order to detect H. bilishepatobiliary diseases.
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