Literature DB >> 28676969

Genetic study of the PAH locus in the Iranian population: familial gene mutations and minihaplotypes.

Masoumeh Razipour1, Elaheh Alavinejad1, Seyede Zahra Sajedi2,3, Saeed Talebi1, Mona Entezam1, Neda Mohajer1, Golnaz-Ensieh Kazemi-Sefat1,4, Jalal Gharesouran3, Aria Setoodeh5, Seyyed Mojtaba Mohaddes Ardebili6,7, Mohammad Keramatipour8.   

Abstract

Phenylketonuria (PKU), one of the most common inborn errors of amino acid metabolism, is caused by mutations in the phenylalanine hydroxylase (PAH) gene (PAH). PKU has wide allelic heterogeneity, and over 600 different disease-causing mutations in PAH have been detected to date. Up to now, there have been no reports on the minihaplotype (VNTR/STR) analysis of PAH locus in the Iranian population. The aims of the present study were to determine PAH mutations and minihaplotypes in Iranian families with PAH deficiency and to investigate the correlation between them. A total of 81 Iranian families with PAH deficiency were examined using PCR-sequencing of all 13 PAH exons and their flanking intron regions to identify sequence variations. Fragment analysis of the PAH minihaplotypes was performed by capillary electrophoresis for 59 families. In our study, 33 different mutations were found accounting for 95% of the total mutant alleles. The majority of these mutations (72%) were distributed across exons 7, 11, 2 and their flanking intronic regions. Mutation c.1066-11G > A was the most common with a frequency of 20.37%. The less frequent mutations, p.Arg261Gln (8%), p.Arg243Ter (7.4%), p.Leu48Ser (7.4%), p.Lys363Asnfs*37 (6.79%), c.969 + 5G > A (6.17%), p.Pro281Leu (5.56), c.168 + 5G > C (5.56), and p.Arg261Ter (4.94) together comprised about 52% of all mutant alleles. In this study, a total of seventeen PAH gene minihaplotypes were detected, six of which associated exclusively with particular mutations. Our findings indicate a broad PAH mutation spectrum in the Iranian population, which is consistent with previous studies reporting a wide range of PAH mutations, most likely due to ethnic heterogeneity. High prevalence of c.1066-11G > A mutation linked to minihaplotype 7/250 among both Iranian and Mediterranean populations is indicative of historical and geographical links between them. Also, strong association between particular mutations and minihaplotypes could be useful for prenatal diagnosis (PND) and preimplantation genetic diagnosis (PGD) in affected families.

Entities:  

Keywords:  Minihaplotype; Mutation; Phenylalanine hydroxylase; Sequencing analysis

Mesh:

Substances:

Year:  2017        PMID: 28676969     DOI: 10.1007/s11011-017-0048-7

Source DB:  PubMed          Journal:  Metab Brain Dis        ISSN: 0885-7490            Impact factor:   3.584


  30 in total

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3.  Phenylketonuria mutations in Germany.

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4.  Phenylketonuria in Iranian population: a study in institutions for mentally retarded in Isfahan.

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Review 7.  Phenylketonuria mutations in Europe.

Authors:  Johannes Zschocke
Journal:  Hum Mutat       Date:  2003-04       Impact factor: 4.878

Review 8.  PAHdb 2003: what a locus-specific knowledgebase can do.

Authors:  Charles R Scriver; Mélanie Hurtubise; David Konecki; Manyphong Phommarinh; Lynne Prevost; Heidi Erlandsen; Ray Stevens; Paula J Waters; Shannon Ryan; David McDonald; Christineh Sarkissian
Journal:  Hum Mutat       Date:  2003-04       Impact factor: 4.878

9.  A Novel Variant in the PAH Gene Causing Phenylketonuria in an Iranian Pedigree.

Authors:  Elaheh Alavinejad; Seyede Zahra Sajedi; Masoumeh Razipour; Mona Entezam; Neda Mohajer; Aria Setoodeh; Saeed Talebi; Mohammad Keramatipour
Journal:  Avicenna J Med Biotechnol       Date:  2017 Jul-Sep

10.  Identification of a Novel Mutation in the PAH Gene in an Iranian Phenylketonuria Family: A Case Report.

Authors:  Masoumeh Razipour; Daniz Kooshavar; Elaheh Alavinejad; Seyede Zahra Sajedi; Neda Mohajer; Aria Setoodeh; Saeed Talebi; Mohammad Keramatipour
Journal:  Iran J Public Health       Date:  2017-04       Impact factor: 1.429

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5.  Molecular-genetic causes for the high frequency of phenylketonuria in the population from the North Caucasus.

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