Literature DB >> 28532645

Identification of a novel PSEN1 mutation (Leu232Pro) in a Korean patient with early-onset Alzheimer's disease and a family history of dementia.

Jiyun Park1, Seong Soo A An2, Vo Van Giau2, Kyuhwan Shim2, Young Chul Youn3, Eva Bagyinszky4, SangYun Kim5.   

Abstract

In the present study, a novel mutation in exon 7 of presenilin 1 (Leu232Pro) was discovered in a Korean patient with early-onset Alzheimer's disease, who represented memory decline at 37 years of age, followed by impairment in spatial activity and concentrations and personality changes. Imaging analyses with magnetic resonance scan showed diffuse atrophy in the frontoparietal regions. Targeted next generation sequencing and Sanger sequencing identified a heterozygous T to C transition at position 695 (c.695T>C) of in presenilin 1 gene (PSEN1), resulting in a novel missense mutation at codon 232 from leucine to proline (L232P). Several family members of the patient developed dementia, suggesting an autosomal dominant inheritance; however, we were unable to perform a segregation analysis to confirm this. Since the proline may play a role as a helix breaker, this mutation could significantly disturb the transmembrane helix domain-V of PSEN1 and perturb its protein functions. This hypothesis was supported by the results from the in silico analyses, predicted a major kink on this helix. Several leucine>proline substitutions in other PSEN1 transmembrane helices revealed aggressive AD phenotypes. Future functional studies would be needed to evaluate the pathogenicity of this mutation in AD.
Copyright © 2017 Elsevier Inc. All rights reserved.

Entities:  

Keywords:  Alzheimer's disease; L232P mutation; Next generation sequencing; Presenilin 1

Mesh:

Substances:

Year:  2017        PMID: 28532645     DOI: 10.1016/j.neurobiolaging.2017.04.012

Source DB:  PubMed          Journal:  Neurobiol Aging        ISSN: 0197-4580            Impact factor:   4.673


  4 in total

1.  A pathogenic PSEN1 Trp165Cys mutation associated with early-onset Alzheimer's disease.

Authors:  Vo Van Giau; Jung-Min Pyun; Jeewon Suh; Eva Bagyinszky; Seong Soo A An; Sang Yun Kim
Journal:  BMC Neurol       Date:  2019-08-07       Impact factor: 2.474

2.  APP, PSEN1, and PSEN2 Mutations in Asian Patients with Early-Onset Alzheimer Disease.

Authors:  Vo Van Giau; Eva Bagyinszky; Young Chul Youn; Seong Soo A An; SangYun Kim
Journal:  Int J Mol Sci       Date:  2019-09-25       Impact factor: 5.923

Review 3.  Amyloid-beta peptide and tau protein crosstalk in Alzheimer's disease.

Authors:  Alejandro R Roda; Gabriel Serra-Mir; Laia Montoliu-Gaya; Lidia Tiessler; Sandra Villegas
Journal:  Neural Regen Res       Date:  2022-08       Impact factor: 5.135

4.  Pathogenic PSEN1 Thr119Ile Mutation in Two Korean Patients with Early-Onset Alzheimer's Disease.

Authors:  Eva Bagyinszky; Hyon Lee; Jung Min Pyun; Jeewon Suh; Min Ju Kang; Van Giau Vo; Seong Soo A An; Kee Hyung Park; SangYun Kim
Journal:  Diagnostics (Basel)       Date:  2020-06-14
  4 in total

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