| Literature DB >> 28495692 |
Pierre-Antoine Juge1,2,3, Raphaël Borie2,4,5,3, Caroline Kannengiesser2,6,7,3, Steven Gazal2,8,9, Patrick Revy10,11, Lidwine Wemeau-Stervinou12,13, Marie-Pierre Debray2,14, Sébastien Ottaviani1,2, Sylvain Marchand-Adam15,16,17, Nadia Nathan18,19,20, Gabriel Thabut2,5,21, Christophe Richez22,23,24, Hilario Nunes25,26, Isabelle Callebaut20,27, Aurélien Justet2,4, Nicolas Leulliot11,28, Amélie Bonnefond13,29,30, David Salgado31,32, Pascal Richette2,33,34, Jean-Pierre Desvignes31,32, Huguette Lioté35, Philippe Froguel13,29,36, Yannick Allanore11,37,38, Olivier Sand13,29,30, Claire Dromer24,39, René-Marc Flipo13,40, Annick Clément18,19,20, Christophe Béroud31,32,41, Jean Sibilia42,43,44, Baptiste Coustet1,2, Vincent Cottin45,46, Marie-Christophe Boissier26,47,48, Benoit Wallaert12,13, Thierry Schaeverbeke22,23,24, Florence Dastot le Moal18,20,49, Aline Frazier2,33, Christelle Ménard18,19,20, Martin Soubrier50, Nathalie Saidenberg26,48, Dominique Valeyre25,26, Serge Amselem18,19,49, Catherine Boileau2,6,51, Bruno Crestani2,4,5, Philippe Dieudé52,2,7.
Abstract
Despite its high prevalence and mortality, little is known about the pathogenesis of rheumatoid arthritis-associated interstitial lung disease (RA-ILD). Given that familial pulmonary fibrosis (FPF) and RA-ILD frequently share the usual pattern of interstitial pneumonia and common environmental risk factors, we hypothesised that the two diseases might share additional risk factors, including FPF-linked genes. Our aim was to identify coding mutations of FPF-risk genes associated with RA-ILD.We used whole exome sequencing (WES), followed by restricted analysis of a discrete number of FPF-linked genes and performed a burden test to assess the excess number of mutations in RA-ILD patients compared to controls.Among the 101 RA-ILD patients included, 12 (11.9%) had 13 WES-identified heterozygous mutations in the TERT, RTEL1, PARN or SFTPC coding regions. The burden test, based on 81 RA-ILD patients and 1010 controls of European ancestry, revealed an excess of TERT, RTEL1, PARN or SFTPC mutations in RA-ILD patients (OR 3.17, 95% CI 1.53-6.12; p=9.45×10-4). Telomeres were shorter in RA-ILD patients with a TERT, RTEL1 or PARN mutation than in controls (p=2.87×10-2).Our results support the contribution of FPF-linked genes to RA-ILD susceptibility.Entities:
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Year: 2017 PMID: 28495692 DOI: 10.1183/13993003.02314-2016
Source DB: PubMed Journal: Eur Respir J ISSN: 0903-1936 Impact factor: 16.671