Literature DB >> 28249924

Whole Exome Sequencing Identifies a Novel Mutation in the PITX3 Gene, Causing Autosomal Dominant Congenital Cataracts in a Chinese Family.

Hui Liu1, Hankui Liu2, Junxiang Tang1, Qiongfen Lin2, Yuxiu Sun1, Chaohong Wang1, Huanming Yang2, Muhammad Riaz Khan3, Mohamud Walid Peerbux4, Sohail Ahmad4, Ihtisham Bukhari5,6, Jiansheng Zhu7.   

Abstract

BACKGROUND: Congenital cataract is the cloudiness of the eye's natural lens and is a primary cause of congenital vision loss. It accounts for almost 10% of childhood vision loss worldwide.
METHODS: A four generation Chinese family having seven affected individuals was recruited for the current study. Exome sequencing was performed to identify the genetic cause of congenital cataract.
RESULTS: Analysis of data identified a novel frameshift mutation, c.608delC (p.A203fs), in the PITX3 gene. This mutation was only observed in the affected individuals while the unaffected members of the family as well as 100 ethnically matched normal controls did not contain this deletion.
CONCLUSION: These findings suggest that p.A203fs is the cause of cataracts in the recruited family. This information would be further helpful in the genetic diagnosis of cataract and in the genetic counseling of similar patients.
© 2017 by the Association of Clinical Scientists, Inc.

Entities:  

Keywords:  Blindness; Cataract; Frame-shift Mutation; PITX3 gene; Vision loss

Mesh:

Substances:

Year:  2017        PMID: 28249924

Source DB:  PubMed          Journal:  Ann Clin Lab Sci        ISSN: 0091-7370            Impact factor:   1.256


  6 in total

Review 1.  Pitx genes in development and disease.

Authors:  Thai Q Tran; Chrissa Kioussi
Journal:  Cell Mol Life Sci       Date:  2021-04-12       Impact factor: 9.261

Review 2.  Mutation update of transcription factor genes FOXE3, HSF4, MAF, and PITX3 causing cataracts and other developmental ocular defects.

Authors:  Deepti Anand; Smriti A Agrawal; Anne Slavotinek; Salil A Lachke
Journal:  Hum Mutat       Date:  2018-01-16       Impact factor: 4.878

Review 3.  Screening, genetics, risk factors, and treatment of neonatal cataracts.

Authors:  Jinyu Li; Chun-Hong Xia; Eddie Wang; Ke Yao; Xiaohua Gong
Journal:  Birth Defects Res       Date:  2017-05-22       Impact factor: 2.661

4.  Association of FOXE3-p.Ala170Ala and PITX3-p.Ile95Ile Polymorphisms with Congenital Cataract and Microphthalmia.

Authors:  Nair Gopinathan Vidya; Darshini Ganatra; Abhay R Vasavada; Sankaranarayanan Rajkumar
Journal:  J Ophthalmic Vis Res       Date:  2018 Oct-Dec

5.  PITX3 mutations associated with autosomal dominant congenital cataract in the Chinese population.

Authors:  Zehua Wu; Delong Meng; Chengbo Fang; Jian Li; Xiujie Zheng; Jiansuo Lin; Haijiang Zeng; Sihan Lv; Zhenning Zhang; Bing Luan; Zilin Zhong; Jianjun Chen
Journal:  Mol Med Rep       Date:  2019-02-26       Impact factor: 2.952

6.  Unilateral buphthalmos, corneal staphyloma and corneal fistula caused by pathogenic variant in the PITX3 gene: a case report.

Authors:  Lin Zhou; Zhike Xu; Qianying Wu; Xin Wei
Journal:  BMC Ophthalmol       Date:  2022-09-24       Impact factor: 2.086

  6 in total

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