Literature DB >> 28027687

ASXL1 mutations in myeloid neoplasms: pathogenetic considerations, impact on clinical outcomes and survival.

Juliana Alvarez Argote1, Constantin A Dasanu2.   

Abstract

BACKGROUND: ASXL1 gene mutations include nonsense, missense, and frameshift mutations. Although their clinical significance is still debated, they may play an important role in the pathogenesis of several hematologic malignancies.
METHODS: Herein, we offer a comprehensive review on ASXL1 mutations, and link them with survival and clinical outcomes in patients with various myeloid neoplasms. Most relevant publications were identified through searching the PubMed/Medline database for articles published from inception to February 2016.
FINDINGS: In acute myeloid leukemia (AML), ASXL1 mutations tend to correlate with older age and male gender, and affect predominantly patients with secondary AML. De novo AML patients with ASXL1 mutations had significantly lower complete remission rates after standard high-dose chemotherapy and shorter survival. In chronic myelomonocytic leukemia and low- or intermediate-risk myelodysplastic syndromes, frameshift and nonsense mutations correlated with shorter survival and a higher risk of leukemic transformation. Overall survival was also shorter in primary myelofibrosis in the presence of ASXL1 mutations.
CONCLUSIONS: Further research on the role of ASXL1 mutations and therapeutic implications in neoplastic myeloid disorders is stringently needed. Given the relatively high prevalence of ASXL1 mutations, larger studies involving patients affected by these mutations will be feasible in the near future.

Entities:  

Keywords:  AML; ASXL1; ASXL1 mutation; Acute myeloid neoplasms; MDS; myelodysplastic syndrome; myeloid neoplasms

Mesh:

Substances:

Year:  2017        PMID: 28027687     DOI: 10.1080/03007995.2016.1276896

Source DB:  PubMed          Journal:  Curr Med Res Opin        ISSN: 0300-7995            Impact factor:   2.580


  10 in total

1.  Familial and Somatic BAP1 Mutations Inactivate ASXL1/2-Mediated Allosteric Regulation of BAP1 Deubiquitinase by Targeting Multiple Independent Domains.

Authors:  Hongzhuang Peng; Jeremy Prokop; Jayashree Karar; Kyewon Park; Li Cao; J William Harbour; Anne M Bowcock; S Bruce Malkowicz; Mitchell Cheung; Joseph R Testa; Frank J Rauscher
Journal:  Cancer Res       Date:  2017-12-28       Impact factor: 12.701

2.  EBV-Negative Monomorphic B-Cell Posttransplant Lymphoproliferative Disorder with Marked Morphologic Pleomorphism and Pathogenic Mutations in ASXL1, BCOR, CDKN2A, NF1, and TP53.

Authors:  Agata M Bogusz
Journal:  Case Rep Hematol       Date:  2017-04-10

3.  Association of mutations with morphological dysplasia in de novo acute myeloid leukemia without 2016 WHO Classification-defined cytogenetic abnormalities.

Authors:  Olga K Weinberg; Christopher J Gibson; Traci M Blonquist; Donna Neuberg; Olga Pozdnyakova; Frank Kuo; Benjamin L Ebert; Robert P Hasserjian
Journal:  Haematologica       Date:  2018-01-11       Impact factor: 9.941

4.  Acute pro-B-Cell lymphoblastic leukemia transformed from myelodysplastic syndrome with an ASXL1 missense mutation: A case report with literature review.

Authors:  Zhi-Ping Guo; Yan-Hong Tan; Jian-Lan Li; Zhi-Fang Xu; Xiu-Hua Chen; Lian-Rong Xu
Journal:  Oncol Lett       Date:  2018-04-20       Impact factor: 2.967

5.  The assessment of minimal residual disease versus that of somatic mutations for predicting the outcome of acute myeloid leukemia patients.

Authors:  Mario Petrini; Sara Galimberti; Serena Salehzadeh; Francesca Guerrini; Umberto Pizzano; Susanna Grassi; Elena Ciabatti; Lorenzo Iovino; Gabriele Buda; Francesco Caracciolo; Edoardo Benedetti; Enrico Orciuolo; Matteo Pelosini; Giovanni Consani; Giovanni Carulli; Maria Rita Metelli; Francesca Martini; Francesco Mazziotta; Elisa Mazzantini; Pietro Rossi; Rita Tavarozzi; Federica Ricci
Journal:  Cancer Cell Int       Date:  2019-04-04       Impact factor: 5.722

6.  Ruxolitinib Reduces Oxidative Stress in Patients With Primary Myelofibrosis: A Multicenter Study.

Authors:  Mahmut B Koyuncu; Mustafa Ilgan; Hakan Basir; Anil Tombak; Mehmet Ali Ucar; Tolga Koseci; Aydan Akdeniz; Eyup N Tiftik; Özcan Erel
Journal:  Cureus       Date:  2022-01-04

Review 7.  ASXL1/2 mutations and myeloid malignancies.

Authors:  Edward A Medina; Caroline R Delma; Feng-Chun Yang
Journal:  J Hematol Oncol       Date:  2022-09-06       Impact factor: 23.168

Review 8.  Targeting histone methyltransferase and demethylase in acute myeloid leukemia therapy.

Authors:  Germana Castelli; Elvira Pelosi; Ugo Testa
Journal:  Onco Targets Ther       Date:  2017-12-28       Impact factor: 4.147

9.  Mutant ASXL1 cooperates with BAP1 to promote myeloid leukaemogenesis.

Authors:  Shuhei Asada; Susumu Goyama; Daichi Inoue; Shiori Shikata; Reina Takeda; Tsuyoshi Fukushima; Taishi Yonezawa; Takeshi Fujino; Yasutaka Hayashi; Kimihito Cojin Kawabata; Tomofusa Fukuyama; Yosuke Tanaka; Akihiko Yokoyama; Satoshi Yamazaki; Hiroko Kozuka-Hata; Masaaki Oyama; Shinya Kojima; Masahito Kawazu; Hiroyuki Mano; Toshio Kitamura
Journal:  Nat Commun       Date:  2018-07-16       Impact factor: 14.919

Review 10.  Landscape of Tumor Suppressor Mutations in Acute Myeloid Leukemia.

Authors:  Cristina Panuzzo; Elisabetta Signorino; Chiara Calabrese; Muhammad Shahzad Ali; Jessica Petiti; Enrico Bracco; Daniela Cilloni
Journal:  J Clin Med       Date:  2020-03-16       Impact factor: 4.241

  10 in total

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