| Literature DB >> 28005197 |
Andreea Manole1,2, Alejandro Horga1, Josep Gamez3, Nuria Raguer4, Maria Salvado5, Beatriz San Millán6, Carmen Navarro6, Alan Pittmann2, Mary M Reilly1, Henry Houlden1,2.
Abstract
Biallelic mutations in the SBF1 gene have been identified in one family with demyelinating Charcot-Marie-Tooth disease (CMT4B3) and two families with axonal neuropathy and additional neurological and skeletal features. Here we describe novel sequence variants in SBF1 (c.1168C>G and c.2209_2210del) as the potential causative mutations in two siblings with severe axonal neuropathy, hearing loss, facial weakness and bulbar features. Pathogenicity of these variants is supported by co-segregation and in silico analyses and evolutionary conservation. Our findings suggest that SBF1 mutations may cause a syndromic form of autosomal recessive axonal neuropathy (AR-CMT2) in addition to CMT4B3.Entities:
Keywords: Charcot-Marie-Tooth disease; Inherited neuropathy; MTMR2; SBF1; SBF2; Whole-exome sequencing
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Year: 2016 PMID: 28005197 DOI: 10.1007/s10048-016-0505-1
Source DB: PubMed Journal: Neurogenetics ISSN: 1364-6745 Impact factor: 2.660