| Literature DB >> 27733599 |
Harvy Mauricio Velasco1, Yasmin Sanchez2, Angela Milena Martin3, Luis A Umaña4.
Abstract
Mucopolysaccharidosis type III, or Sanfilippo syndrome, is an autosomal recessive disorder characterized by impairment in the degradation of Heparan sulfate. Here the authors describe the natural history of 5 related individuals; all associated through a large pedigree which reports a total of 11 affected members, originally from the Boyacá region in Colombia, diagnosed with MPS IIIC who all harbor a novel mutation in HGSNAT. The authors report an unusually high incidence of the disease in this population. The clinical features are similar to previously described patients, although some differences in the degree of severity and end-stage of the disease are seen in this specific group. The authors consider that the high degree of endogamy in this specific population could underlie modifying factors for the severity of presentation in these patients. Future studies might provide more information on the functional effect of this novel mutation, which could define this group as a genetic isolate.Entities:
Keywords: Mucopolysaccharidosis IIIC; disease progression; endophenotype; lysosomal storage disease; neurocognitive disorder
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Year: 2016 PMID: 27733599 DOI: 10.1177/0883073816672391
Source DB: PubMed Journal: J Child Neurol ISSN: 0883-0738 Impact factor: 1.987