| Literature DB >> 27566612 |
Wenjun Mou1,2, Jianxin He1,3, Xi Chen1,2, Hui Zhang1,2, Xiaoya Ren1,2, Xunyao Wu1,2, Xin Ni1,4, Baoping Xu1,3, Jingang Gui5,6.
Abstract
Severe combined immunodeficiency (SCID) is the most serious disorder among primary immunodeficiency diseases threatening children's life. Atypical SCID variant, presenting with mild reduced T cells subsets, is often associated with infection susceptibility but poor clinical diagnosis. The atypical X-SCID patient in the present study showed a mild clinical presentation with a TlowNK+B+ immunophenotype. The patient has reduced T- cell subpopulations with a subdued thymic output measured by sjTRECs. Further analysis showed that T cells maintained a normal proliferation and a broad Vβ repertoire. NK cells, however, exhibited a skewed development toward immature CD3-CD16+CD56- cells. Genetic analysis revealed a novel deletion at nucleotide 52 in exon 1 of IL2RG gene. Sequence alignment predicted a truncated IL2RG protein missing signal peptide derived from a possible alternative reading frame. The novel mutation in IL2RG gene identified in our study may help the early diagnosis of atypical X-SCID.Entities:
Keywords: Atypical SCID; Frameshift; IL2RG gene; Primary immunodeficiency diseases; Signal peptide; X-linked SCID
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Year: 2016 PMID: 27566612 DOI: 10.1007/s00251-016-0949-3
Source DB: PubMed Journal: Immunogenetics ISSN: 0093-7711 Impact factor: 2.846