Literature DB >> 27493320

Zellweger syndrome: A cause of neonatal hypotonia and seizures.

Abdelmoneim E M Kheir1.   

Abstract

Zellweger syndrome, a paradigm of human peroxisomal disorders is characterized by dysmorphic features, hypotonia, severe neuro-developmental delay, hepatomegaly, renal cysts, sensorineural deafness and retinal dysfunction. This is a case report of a baby boy born with facial dysmorphism, profound hypotonia, seizures, and hepatomegaly. The diagnosis was not evident initially but only later when he presented with obstructive jaundiced and renal cysts. He died at the age of seven months. Biochemical studies revealed elevation of very long chain fatty acids and phytanic acid consistent with a peroxisomal disorder. The recognition of this syndrome is important since it is a fatal hereditary disease. Zellweger syndrome should be included in the differential diagnosis of infantile hypotonia and dysmorphism.

Entities:  

Keywords:  Child; Peroxisomal disorders; Zellweger syndrome

Year:  2011        PMID: 27493320      PMCID: PMC4949836     

Source DB:  PubMed          Journal:  Sudan J Paediatr        ISSN: 0256-4408


  13 in total

Review 1.  Biochemistry of peroxisomes.

Authors:  H van den Bosch; R B Schutgens; R J Wanders; J M Tager
Journal:  Annu Rev Biochem       Date:  1992       Impact factor: 23.643

2.  A FAMILIAL SYNDROME OF MULTIPLE CONGENITAL DEFECTS.

Authors:  P BOWEN; C S LEE; H ZELLWEGER; R LINDENBERG
Journal:  Bull Johns Hopkins Hosp       Date:  1964-06

Review 3.  Zellweger syndrome and associated phenotypes.

Authors:  D R FitzPatrick
Journal:  J Med Genet       Date:  1996-10       Impact factor: 6.318

Review 4.  Peroxisome biogenesis disorders.

Authors:  Steven J Steinberg; Gabriele Dodt; Gerald V Raymond; Nancy E Braverman; Ann B Moser; Hugo W Moser
Journal:  Biochim Biophys Acta       Date:  2006-09-14

5.  The evaluation of infants with the Zellweger (cerebro-hepato-renal) syndrome.

Authors:  K W Gilchrist; E F Gilbert; N T Shahidi; J M Opitz
Journal:  Clin Genet       Date:  1975 May-Jun       Impact factor: 4.438

6.  Peroxisomal and mitochondrial defects in the cerebro-hepato-renal syndrome.

Authors:  S Goldfischer; C L Moore; A B Johnson; A J Spiro; M P Valsamis; H K Wisniewski; R H Ritch; W T Norton; I Rapin; L M Gartner
Journal:  Science       Date:  1973-10-05       Impact factor: 47.728

7.  Clinical, biochemical and molecular characterization of peroxisomal diseases in Arabs.

Authors:  R Shaheen; O Y Al-Dirbashi; Z N Al-Hassnan; M Al-Owain; N Makhsheed; F Basheeri; M Z Seidahmed; M A M Salih; E Faqih; H Zaidan; M Al-Sayed; Z Rahbeeni; T Al-Sheddi; M Hashem; W Kurdi; N Shimozawa; F S Alkuraya
Journal:  Clin Genet       Date:  2011-01       Impact factor: 4.438

Review 8.  Peroxisomal disorders: a review.

Authors:  B Fournier; J A Smeitink; L Dorland; R Berger; J M Saudubray; B T Poll-The
Journal:  J Inherit Metab Dis       Date:  1994       Impact factor: 4.982

9.  Zellweger syndrome caused by PEX13 deficiency: report of two novel mutations.

Authors:  O Y Al-Dirbashi; R Shaheen; M Al-Sayed; M Al-Dosari; N Makhseed; L Abu Safieh; T Santa; B F Meyer; N Shimozawa; F S Alkuraya
Journal:  Am J Med Genet A       Date:  2009-06       Impact factor: 2.802

10.  Mutations in the 70K peroxisomal membrane protein gene in Zellweger syndrome.

Authors:  J Gärtner; H Moser; D Valle
Journal:  Nat Genet       Date:  1992-04       Impact factor: 38.330

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.