Literature DB >> 2744041

Fatal neonatal cardiomyopathy associated with cataract and mitochondrial myopathy.

J A Smeitink1, R C Sengers, J M Trijbels, W Ruitenbeek, O Daniëls, A M Stadhouders, M J Kock-Jansen.   

Abstract

Three patients suffering from the neonatal form of a syndrome characterized by congenital cataract, hypertrophic cardiomyopathy, and mitochondrial myopathy are described. The patients died at 7, 10 and 18 days, respectively from cardiorespiratory failure. Mitochondrial abnormalities were observed in the heart and skeletal muscle. Despite the presence of a severe lactic acidaemia pointing to a disturbed pyruvate oxidation rate in vivo, a normal pyruvate oxidation rate was demonstrated in skeletal muscle homogenates. The activities of several enzymes of the mitochondrial respiratory chain appeared to be normal, indicating an intact respiratory chain. A myoglobinopenia could be excluded. The activities of some mitochondrial enzymes and the concentration of myoglobin increase with age.

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Year:  1989        PMID: 2744041     DOI: 10.1007/bf00441527

Source DB:  PubMed          Journal:  Eur J Pediatr        ISSN: 0340-6199            Impact factor:   3.183


  14 in total

1.  Congenital cataract and mitochondrial myopathy of skeletal and heart muscle associated with lactic acidosis after exercise.

Authors:  R C Sengers; J M Trijbels; J L Willems; O Daniels; A M Stadhouders
Journal:  J Pediatr       Date:  1975-06       Impact factor: 4.406

2.  The asymmetrically hypertrophied septum. Further differentiation of its causes.

Authors:  W E Larter; H D Allen; D J Sahn; S J Goldberg
Journal:  Circulation       Date:  1976-01       Impact factor: 29.690

3.  Measurement of cytochromes in human skeletal muscle mitochondria, isolated from fresh and frozen stored muscle specimens.

Authors:  H Bookelman; J M Trijbels; R C Sengers; A J Janssen
Journal:  Biochem Med       Date:  1978-06

4.  Of men and mitochondria: coping with hypoxic dysoxia. The 1980 J. Burns Amberson Lecture.

Authors:  E D Robin
Journal:  Am Rev Respir Dis       Date:  1980-10

5.  Hypertrophic cardiomyopathy associated with a mitochondrial myopathy of voluntary muscles and congenital cataract.

Authors:  R C Sengers; A M Stadhouders; E van Lakwijk-Vondrovicova; K Kubat; W Ruitenbeek
Journal:  Br Heart J       Date:  1985-11

6.  Features of a syndrome with congenital cataract and hypertrophic cardiomyopathy.

Authors:  J R Cruysberg; R C Sengers; A Pinckers; K Kubat; U J van Haelst
Journal:  Am J Ophthalmol       Date:  1986-12-15       Impact factor: 5.258

Review 7.  Oxidative stress on lens and cataract formation: role of light and oxygen.

Authors:  S D Varma; D Chand; Y R Sharma; J F Kuck; R D Richards
Journal:  Curr Eye Res       Date:  1984-01       Impact factor: 2.424

8.  Myoglobin in human skeletal muscle.

Authors:  P Möller; C Sylvén
Journal:  Scand J Clin Lab Invest       Date:  1981-09       Impact factor: 1.713

9.  A mitochondrial encephalomyopathy: the first case with an established defect at the level of coenzyme Q.

Authors:  J C Fischer; W Ruitenbeek; F J Gabreëls; A J Janssen; W O Renier; R C Sengers; A M Stadhouders; H J ter Laak; J M Trijbels; J H Veerkamp
Journal:  Eur J Pediatr       Date:  1986-02       Impact factor: 3.183

10.  Hypertrophic cardiomyopathy in infants: clinical features and natural history.

Authors:  B J Maron; A J Tajik; H D Ruttenberg; T P Graham; G F Atwood; B E Victorica; J T Lie; W C Roberts
Journal:  Circulation       Date:  1982-01       Impact factor: 29.690

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  11 in total

Review 1.  Human mitochondrial complex I in health and disease.

Authors:  J Smeitink; L van den Heuvel
Journal:  Am J Hum Genet       Date:  1999-06       Impact factor: 11.025

2.  Mutation in the AGK gene in two siblings with unusual Sengers syndrome.

Authors:  Sanae Allali; Imen Dorboz; Simon Samaan; Abdelhamid Slama; Charlène Rambaud; Odile Boespflug-Tanguy; Catherine Sarret
Journal:  Metab Brain Dis       Date:  2017-09-03       Impact factor: 3.584

3.  Biochemical parameters for the diagnosis of mitochondrial respiratory chain deficiency in humans, and their lack of age-related changes.

Authors:  D Chretien; J Gallego; A Barrientos; J Casademont; F Cardellach; A Munnich; A Rötig; P Rustin
Journal:  Biochem J       Date:  1998-01-15       Impact factor: 3.857

4.  Fatal infantile mitochondrial cardiomyopathy and myopathy with heterogeneous tissue expression of combined respiratory chain deficiencies.

Authors:  J Müller-Höcker; H Ibel; I Paetzke; T Deufel; W Endres; B Kadenbach; J M Gokel; G Hübner
Journal:  Virchows Arch A Pathol Anat Histopathol       Date:  1991

Review 5.  A retrospective study of patients with the hereditary syndrome of congenital cataract, mitochondrial myopathy of heart and skeletal muscle and lactic acidosis.

Authors:  G J van Ekeren; A M Stadhouders; J A Smeitink; R C Sengers
Journal:  Eur J Pediatr       Date:  1993-03       Impact factor: 3.183

6.  Sengers disease: a rare association of hypertrophic cardiomyopathy and congenital cataracts.

Authors:  Mehnaz Atiq; S Iqbal; S Ibrahim
Journal:  Indian J Pediatr       Date:  2004-05       Impact factor: 1.967

7.  Congenital hypertrophic cardiomyopathy, cataract, mitochondrial myopathy and defective oxidative phosphorylation in two siblings with Sengers-like syndrome.

Authors:  Eva Morava; Rob Sengers; Henk Ter Laak; Lambert Van Den Heuvel; Antoon Janssen; Frans Trijbels; Hans Cruysberg; Carolien Boelen; Jan Smeitink
Journal:  Eur J Pediatr       Date:  2004-05-27       Impact factor: 3.183

8.  Lack of the mitochondrial protein acylglycerol kinase causes Sengers syndrome.

Authors:  Johannes A Mayr; Tobias B Haack; Elisabeth Graf; Franz A Zimmermann; Thomas Wieland; Birgit Haberberger; Andrea Superti-Furga; Janbernd Kirschner; Beat Steinmann; Matthias R Baumgartner; Isabella Moroni; Eleonora Lamantea; Massimo Zeviani; Richard J Rodenburg; Jan Smeitink; Tim M Strom; Thomas Meitinger; Wolfgang Sperl; Holger Prokisch
Journal:  Am J Hum Genet       Date:  2012-01-26       Impact factor: 11.025

9.  Human mitochondrial transmembrane metabolite carriers: tissue distribution and its implication for mitochondrial disorders.

Authors:  M Huizing; W Ruitenbeek; L P van den Heuvel; V Dolce; V Iacobazzi; J A Smeitink; F Palmieri; J M Trijbels
Journal:  J Bioenerg Biomembr       Date:  1998-06       Impact factor: 2.945

Review 10.  Disorders of phospholipid metabolism: an emerging class of mitochondrial disease due to defects in nuclear genes.

Authors:  Ya-Wen Lu; Steven M Claypool
Journal:  Front Genet       Date:  2015-02-03       Impact factor: 4.599

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