Literature DB >> 27334242

Acrodermatitis dysmetabolica in an infant with maple syrup urine disease.

K Flores1, R Chikowski1, D S Morrell1.   

Abstract

Acrodermatitis dysmetabolica (AD) is a rare, newly termed, and poorly understood disease that appears to be clinically similar to acrodermatitis enteropathica (AE). Both diseases are characterized by the triad of periorificial and acral dermatitis, diarrhoea, and alopecia. Unlike AE, which is caused by zinc deficiency, AD is caused by numerous metabolic disorders. One such disorder is maple syrup urine disease (MSUD), a genetic deficiency of branched chain α-ketoacid dehydrogenase, the enzyme that degrades the branched-chain amino acids (BCAAs) isoleucine, leucine and valine. Treatment involves restricting BCAAs to prevent accumulation. We report a case of an infant being treated for MSUD, who developed the triad of AE/AD after a period of poor BCAA formula intake. The child was found to have low isoleucine and normal zinc levels. Increasing the isoleucine dose improved the eruption, thus the diagnosis of AD secondary to isoleucine deficiency was made. This case emphasizes the importance of carefully balancing BCAA levels while treating MSUD, as deficiency can precipitate AD.
© 2016 British Association of Dermatologists.

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Year:  2016        PMID: 27334242     DOI: 10.1111/ced.12876

Source DB:  PubMed          Journal:  Clin Exp Dermatol        ISSN: 0307-6938            Impact factor:   3.470


  4 in total

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3.  Natural history of children and adults with maple syrup urine disease in the NBS-MSUD Connect registry.

Authors:  Aileen Kenneson; Yetsa Osara; Theresa Pringle; Lauren Youngborg; Rani H Singh
Journal:  Mol Genet Metab Rep       Date:  2018-01-28

4.  Skin Lesions Associated with Nutritional Management of Maple Syrup Urine Disease.

Authors:  Jaraspong Uaariyapanichkul; Puthita Saengpanit; Ponghatai Damrongphol; Kanya Suphapeetiporn; Sirinuch Chomtho
Journal:  Case Rep Dermatol Med       Date:  2017-10-25
  4 in total

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