Literature DB >> 27311568

Identification of C12orf4 as a gene for autosomal recessive intellectual disability.

A K Philips1, M Pinelli2,3, C I de Bie4, A Mustonen5, T Määttä6, H H Arts7,8, K Wu7, R Roepman7, J S Moilanen5, S Raza1, T Varilo1, G Scala9, S Cocozza9, C Gilissen2, K L I van Gassen4, I Järvelä1.   

Abstract

Intellectual disability (ID) is a major health problem in our society. Genetic causes of ID remain unknown because of its vast heterogeneity. Here we report two Finnish families and one Dutch family with affected individuals presenting with mild to moderate ID, neuropsychiatric symptoms and delayed speech development. By utilizing whole exome sequencing (WES), we identified a founder missense variant c.983T>C (p.Leu328Pro) in seven affected individuals from two Finnish consanguineous families and a deletion c.799_1034-429delinsTTATGA (p.Gln267fs) in one affected individual from a consanguineous Dutch family in the C12orf4 gene on chromosome 12. Both the variants co-segregated in the respective families as an autosomal recessive trait. Screening of the p.Leu328Pro variant showed enrichment in the North Eastern sub-isolate of Finland among anonymous local blood donors with a carrier frequency of 1:53, similar to other disease mutations with a founder effect in that region. To date, only one Arab family with a three affected individuals with a frameshift insertion variant in C12orf4 has been reported. In summary, we expand and establish the clinical and mutational spectrum of C12orf4 variants. Our findings implicate C12orf4 as a causative gene for autosomal recessive ID.
© 2016 John Wiley & Sons A/S. Published by John Wiley & Sons Ltd.

Entities:  

Keywords:  C12orf4; founder effect; frameshift variant; intellectual disability; missense variant; whole exome sequencing

Mesh:

Substances:

Year:  2016        PMID: 27311568     DOI: 10.1111/cge.12821

Source DB:  PubMed          Journal:  Clin Genet        ISSN: 0009-9163            Impact factor:   4.438


  6 in total

1.  Mapping autosomal recessive intellectual disability: combined microarray and exome sequencing identifies 26 novel candidate genes in 192 consanguineous families.

Authors:  R Harripaul; N Vasli; A Mikhailov; M A Rafiq; K Mittal; C Windpassinger; T I Sheikh; A Noor; H Mahmood; S Downey; M Johnson; K Vleuten; L Bell; M Ilyas; F S Khan; V Khan; M Moradi; M Ayaz; F Naeem; A Heidari; I Ahmed; S Ghadami; Z Agha; S Zeinali; R Qamar; H Mozhdehipanah; P John; A Mir; M Ansar; L French; M Ayub; J B Vincent
Journal:  Mol Psychiatry       Date:  2017-04-11       Impact factor: 15.992

2.  Spatial Proteomic Approach to Characterize Skeletal Muscle Myofibers.

Authors:  Katherine M Fomchenko; Elise M Walsh; Xiaoping Yang; Rohan X Verma; Brian L Lin; Tim O Nieuwenhuis; Arun H Patil; Karen Fox-Talbot; Matthew N McCall; David A Kass; Avi Z Rosenberg; Marc K Halushka
Journal:  J Proteome Res       Date:  2020-11-30       Impact factor: 4.466

3.  GeneHancer: genome-wide integration of enhancers and target genes in GeneCards.

Authors:  Simon Fishilevich; Ron Nudel; Noa Rappaport; Rotem Hadar; Inbar Plaschkes; Tsippi Iny Stein; Naomi Rosen; Asher Kohn; Michal Twik; Marilyn Safran; Doron Lancet; Dana Cohen
Journal:  Database (Oxford)       Date:  2017-01-01       Impact factor: 3.451

4.  A novel variant of C12orf4 in a consanguineous Armenian family confirms the etiology of autosomal recessive intellectual disability type 66 with delineation of the phenotype.

Authors:  Miroslava Hancarova; Davit Babikyan; Sarka Bendova; Susanna Midyan; Darina Prchalova; Gohar Shahsuvaryan; Viktor Stranecky; Tamara Sarkisian; Zdenek Sedlacek
Journal:  Mol Genet Genomic Med       Date:  2019-07-23       Impact factor: 2.183

5.  Comprehensive multi-omics integration identifies differentially active enhancers during human brain development with clinical relevance.

Authors:  Ruizhi Deng; Kristina Lanko; Eva Medico Salsench; Anita Nikoncuk; Soheil Yousefi; Herma C van der Linde; Elena Perenthaler; Tjakko J van Ham; Eskeatnaf Mulugeta; Tahsin Stefan Barakat
Journal:  Genome Med       Date:  2021-10-19       Impact factor: 11.117

6.  Exome sequencing discloses KALRN homozygous variant as likely cause of intellectual disability and short stature in a consanguineous pedigree.

Authors:  Periklis Makrythanasis; Michel Guipponi; Federico A Santoni; Maha Zaki; Mahmoud Y Issa; Muhammad Ansar; Hanan Hamamy; Stylianos E Antonarakis
Journal:  Hum Genomics       Date:  2016-07-16       Impact factor: 4.639

  6 in total

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