Literature DB >> 27255140

Identification of Cryptic Novel α-Galactosidase A Gene Mutations: Abnormal mRNA Splicing and Large Deletions.

Takashi Higuchi1, Masahisa Kobayashi2, Jin Ogata2, Eiko Kaneshiro2, Yohta Shimada3, Hiroshi Kobayashi3,2, Yoshikatsu Eto4, Shiro Maeda5, Akira Ohtake6, Hiroyuki Ida3,2, Toya Ohashi7,8.   

Abstract

Anderson-Fabry (FD) disease is an inborn error of metabolism caused by a deficiency of α-galactosidase A (GLA), a lysosomal enzyme. Many male FD patients display a classic FD phenotype; however, some female patients have neither reduced leukocyte GLA enzyme activity level nor FD symptoms. Thus, GLA gene analysis is especially important for diagnosing suspected FD in female subjects. In this study, we revealed 4 novel GLA gene mutations in 5 independent families using GLA cDNA analysis and multiplex ligation-dependent probe amplification (MLPA) analysis. These distinct mutations included a large deletion mutation from intron 1 to exon 5 (c.195-471_c.691del5.5k, corresponding to g.8508_g.14069del5.5k), an insertion mutation of splicing enhancer sequence in intron 4 (c.639+329_c.639+330ins113, corresponding to g.12627_g.12628ins113), an insertion mutation of retrotransposon L1 in exon 4 (c.634_c.635, corresponding to g.12293_g.12294), and a non-SNP deep intronic point mutation in intron 3 (c.547+395G>C, corresponding to g.11727G>C). It is difficult to detect these mutations with direct sequencing of only the exonic element. When exonic mutations are not found in the GLA gene from suspected FD patients, GLA cDNA and MLPA analyses should be performed to detect large deletion/insertion and intronic mutations including transcription abnormalities.

Entities:  

Year:  2016        PMID: 27255140      PMCID: PMC5110446          DOI: 10.1007/8904_2015_475

Source DB:  PubMed          Journal:  JIMD Rep        ISSN: 2192-8304


  25 in total

1.  Five novel mutations in fourteen patients with Fabry Disease.

Authors:  K M Rosenberg; R Schiffmann; C Kaneski; R O Brady; S A Sorensen; L Hasholt
Journal:  Hum Mutat       Date:  2000-02       Impact factor: 4.878

2.  A high-throughput SNP typing system for genome-wide association studies.

Authors:  Y Ohnishi; T Tanaka; K Ozaki; R Yamada; H Suzuki; Y Nakamura
Journal:  J Hum Genet       Date:  2001       Impact factor: 3.172

3.  Replication stalling at unstable inverted repeats: interplay between DNA hairpins and fork stabilizing proteins.

Authors:  Irina Voineagu; Vidhya Narayanan; Kirill S Lobachev; Sergei M Mirkin
Journal:  Proc Natl Acad Sci U S A       Date:  2008-07-15       Impact factor: 11.205

4.  Alternative splicing in the alpha-galactosidase A gene: increased exon inclusion results in the Fabry cardiac phenotype.

Authors:  Satoshi Ishii; Shoichiro Nakao; Reiko Minamikawa-Tachino; Robert J Desnick; Jian-Qiang Fan
Journal:  Am J Hum Genet       Date:  2002-02-04       Impact factor: 11.025

5.  A quantitative-PCR protocol rapidly detects αGAL deletions/duplications in patients with Anderson-Fabry disease.

Authors:  Nicola Marziliano; Nadia Sapere; Francesco Orsini; Valentina Motta; Silvio Veronese; Marcello Gambacorta; Piera Angelica Merlini; Mariano Intrieri
Journal:  Mol Genet Metab       Date:  2012-01-21       Impact factor: 4.797

6.  No accumulation of globotriaosylceramide in the heart of a patient with the E66Q mutation in the α-galactosidase A gene.

Authors:  Masahisa Kobayashi; Toya Ohashi; Takahiro Fukuda; Tomoyoshi Yanagisawa; Takayuki Inomata; Takashi Nagaoka; Teruo Kitagawa; Yoshikatsu Eto; Hiroyuki Ida; Eiji Kusano
Journal:  Mol Genet Metab       Date:  2012-10-24       Impact factor: 4.797

7.  A purine-rich intronic element enhances alternative splicing of thyroid hormone receptor mRNA.

Authors:  M L Hastings; C M Wilson; S H Munroe
Journal:  RNA       Date:  2001-06       Impact factor: 4.942

Review 8.  Mobile elements and disease.

Authors:  H H Kazazian
Journal:  Curr Opin Genet Dev       Date:  1998-06       Impact factor: 5.578

9.  Fabry disease: identification of 50 novel alpha-galactosidase A mutations causing the classic phenotype and three-dimensional structural analysis of 29 missense mutations.

Authors:  Junaid Shabbeer; Makiko Yasuda; Stacy D Benson; Robert J Desnick
Journal:  Hum Genomics       Date:  2006-03       Impact factor: 4.639

10.  The NF1 gene contains hotspots for L1 endonuclease-dependent de novo insertion.

Authors:  Katharina Wimmer; Tom Callens; Annekatrin Wernstedt; Ludwine Messiaen
Journal:  PLoS Genet       Date:  2011-11-17       Impact factor: 5.917

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  2 in total

1.  Identification and functional characterization of the first deep intronic GLA mutation (IVS4+1326C>T) causing renal variant of Fabry disease.

Authors:  Xuantong Dai; Xue Zong; Xiaoxia Pan; Wei Lu; Geng-Ru Jiang; Fujun Lin
Journal:  Orphanet J Rare Dis       Date:  2022-06-20       Impact factor: 4.303

2.  Analysis of Pathogenic Pseudoexons Reveals Novel Mechanisms Driving Cryptic Splicing.

Authors:  Niall P Keegan; Steve D Wilton; Sue Fletcher
Journal:  Front Genet       Date:  2022-01-24       Impact factor: 4.772

  2 in total

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