Literature DB >> 27230627

A 16q12.2q21 deletion identified in a patient with developmental delay, epilepsy, short stature, and distinctive features.

Toshiyuki Yamamoto1, Keiko Shimojima1, Sawako Yamazaki2, Kanju Ikeno2,3, Jun Tohyama4.   

Abstract

Interstitial deletions of the 16q centromeric region are rarely reported. A microdeletion of the 16q12.2q21 region was identified in a patient with intellectual disability, epilepsy, short stature, and distinctive features; including up-slanting palpebral fissures, hypertelorism, epicanthic folds, anteverted nares, simple philtrum, thin upper lip vermilion, high arched palate, posteriorly rotated ears, and overlapping toes in his right foot. Although the deleted region includes the genes responsible for neurological impairments (GNOA1, GPR56, KATNB1, and BBS2), haploinsufficiency of these genes would not be associated with the patient's phenotype. When NDRG4, present in the deleted region, was knocked out in mice, these mice exhibited spatial learning deficits. Thus, we hypothesize that this gene could be a potential candidate underlying the neurological observations of the patient. Because RSPRY1 was been discovered as the cause of progressive skeletal dysplasia, a loss of this gene might explain the skeletal defects observed in the patient.
© 2016 Japanese Teratology Society.

Entities:  

Keywords:  16q12.2q21 deletion; NDRG4; RSPRY1; epilepsy; intellectual disability

Mesh:

Year:  2016        PMID: 27230627     DOI: 10.1111/cga.12172

Source DB:  PubMed          Journal:  Congenit Anom (Kyoto)        ISSN: 0914-3505            Impact factor:   1.409


  2 in total

1.  Congenital Heart Defects and Dysmorphic Facial Features in Patients Suspicious of 22q11.2 Deletion Syndrome in Southern Brazil.

Authors:  Bruna Lixinski Diniz; Andressa Schneiders Santos; Andressa Barreto Glaeser; Bruna Baierle Guaraná; Cláudia Fernandes Lorea; Juliana Alves Josahkian; Janaína Huber; Rafael Fabiano Machado Rosa; Paulo Ricardo Gazzola Zen
Journal:  J Pediatr Genet       Date:  2020-06-17

2.  Gitelman syndrome caused by a novel hemiallelic missense mutation in SLC12A3 revealed by 16q12.2q21 microdeletion.

Authors:  Yuki Abe; Toshiyuki Yamamoto; Yukie Izumita; Shinya Tsukano
Journal:  Hum Genome Var       Date:  2020-05-27
  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.