Literature DB >> 27195205

Keratocystic odontogenic tumors related to Gorlin-Goltz syndrome: A clinicopathological study.

Mohammed Israr Ul Khaliq1, Ajaz A Shah2, Irshad Ahmad3, Shahid Hasan3, Sagar S Jangam4.   

Abstract

BACKGROUND: Assess clinicopathological features of patients with keratocystic odontogenic tumor (KCOT) associated with Gorlin-Goltz syndrome in our institution from 2004 to 2015.
METHOD: After histopathological analyses of KCOT related to Gorlin-Goltz syndrome, 7 patients were assessed. These patients presented a total of 15 primary and 2 recurrent KCOT.
RESULTS: All patients presented a multiple KCOT, and 13 lesions were located in mandible (77%) and 4 (23%) in maxilla. Most of the tumors presented a unilocular pattern (71%) and had tooth association (88%). Four patients (57%) were in the age group of 10-19 years and three patients (43%) were in the age group of 20-29 years. There were four male and three female patients.
CONCLUSION: KCOT is a frequent manifestation of Gorlin-Goltz syndrome and can be its first sign, mainly in young patients. The four patients presented with two lesions (57%) and three lesions in three patients (43%).

Entities:  

Keywords:  Gorlin–Goltz syndrome; Keratocyst; Keratocystic odontogenic tumor; Nevoid basal cell carcinoma syndrome

Year:  2015        PMID: 27195205      PMCID: PMC4862113          DOI: 10.1016/j.jobcr.2015.09.002

Source DB:  PubMed          Journal:  J Oral Biol Craniofac Res        ISSN: 2212-4268


  23 in total

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Review 4.  Basal cell nevus syndrome with squamous cell carcinoma of the maxilla: report of a case.

Authors:  K Hasegawa; T Amagasa; S Shioda; T Kayano
Journal:  J Oral Maxillofac Surg       Date:  1989-06       Impact factor: 1.895

5.  Gorlin-Goltz syndrome and neoplasms: a case study.

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6.  Nevoid basal cell carcinoma syndrome. Clinical findings in 37 Italian affected individuals.

Authors:  L Lo Muzio; P F Nocini; A Savoia; U Consolo; M Procaccini; L Zelante; G Pannone; P Bucci; M Dolci; F Bambini; P Solda; G Favia
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8.  The odontogenic keratocyst and its occurrence in the nevoid basal cell carcinoma syndrome.

Authors:  J A Woolgar; J W Rippin; R M Browne
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9.  Gorlin-goltz syndrome.

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10.  Ameloblastoma: a neglected criterion for nevoid basal cell carcinoma (Gorlin) syndrome.

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Authors:  Shoko Onodera; Yuriko Nakamura; Toshifumi Azuma
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