Literature DB >> 27117551

Severe early-onset epileptic encephalopathy due to mutations in the KCNA2 gene: Expansion of the genotypic and phenotypic spectrum.

Khaled Hundallah1, Asma'a Alenizi1, Amal AlHashem2, Brahim Tabarki3.   

Abstract

BACKGROUND: Recently, de novo loss- or gain-of-function mutations in the KCNA2 gene; have been described in individuals with epileptic encephalopathy, ataxia or intellectual disability. CASE DESCRIPTION: In this report, we describe a further case of KCNA2-early-onset epileptic encephalopathy. The patient presented since birth with intractable seizures, progressive microcephaly, developmental delay, and progressive brain atrophy. Whole-exome sequencing showed a novel de novo mutation in the KCNA2 gene: c.1120A > G (p.Thr374Ala).
CONCLUSION: This case expands the genotypic and phenotypic disease spectrum of this genetic form of KCNA2-early onset epileptic encephalopathy.
Copyright © 2016 European Paediatric Neurology Society. Published by Elsevier Ltd. All rights reserved.

Entities:  

Keywords:  Epileptic encephalopathy; KCNA2

Mesh:

Substances:

Year:  2016        PMID: 27117551     DOI: 10.1016/j.ejpn.2016.03.011

Source DB:  PubMed          Journal:  Eur J Paediatr Neurol        ISSN: 1090-3798            Impact factor:   3.140


  9 in total

1.  Dominant KCNA2 mutation causes episodic ataxia and pharmacoresponsive epilepsy.

Authors:  Mark A Corbett; Susannah T Bellows; Melody Li; Renée Carroll; Silvana Micallef; Gemma L Carvill; Candace T Myers; Katherine B Howell; Snezana Maljevic; Holger Lerche; Elena V Gazina; Heather C Mefford; Melanie Bahlo; Samuel F Berkovic; Steven Petrou; Ingrid E Scheffer; Jozef Gecz
Journal:  Neurology       Date:  2016-10-12       Impact factor: 9.910

Review 2.  Ion Channels in Genetic Epilepsy: From Genes and Mechanisms to Disease-Targeted Therapies.

Authors:  Julia Oyrer; Snezana Maljevic; Ingrid E Scheffer; Samuel F Berkovic; Steven Petrou; Christopher A Reid
Journal:  Pharmacol Rev       Date:  2018-01       Impact factor: 25.468

3.  Wwox deletion leads to reduced GABA-ergic inhibitory interneuron numbers and activation of microglia and astrocytes in mouse hippocampus.

Authors:  Tabish Hussain; Hyunsuk Kil; Bharathi Hattiangady; Jaeho Lee; Maheedhar Kodali; Bing Shuai; Sahithi Attaluri; Yoko Takata; Jianjun Shen; Martin C Abba; Ashok K Shetty; C Marcelo Aldaz
Journal:  Neurobiol Dis       Date:  2018-10-02       Impact factor: 5.996

4.  Myoclonic Epilepsy: Case Report of a Mild Phenotype in a Pediatric Patient Expanding Clinical Spectrum of KCNA2 Pathogenic Variants.

Authors:  Lorenzo Perilli; Gioia Mastromoro; Manuel Murciano; Ilaria Amedeo; Federica Avenoso; Antonio Pizzuti; Cristiana Alessia Guido; Alberto Spalice
Journal:  Front Neurol       Date:  2022-02-01       Impact factor: 4.003

5.  Tracking the motion of the KV 1.2 voltage sensor reveals the molecular perturbations caused by a de novo mutation in a case of epilepsy.

Authors:  Antonios Pantazis; Maki Kaneko; Marina Angelini; Federica Steccanella; Annie M Westerlund; Sarah H Lindström; Michelle Nilsson; Lucie Delemotte; Sulagna C Saitta; Riccardo Olcese
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6.  A recurrent mutation in KCNA2 as a novel cause of hereditary spastic paraplegia and ataxia.

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Journal:  Ann Neurol       Date:  2016-09-09       Impact factor: 10.422

7.  Slc7a5 regulates Kv1.2 channels and modifies functional outcomes of epilepsy-linked channel mutations.

Authors:  Victoria A Baronas; Runying Y Yang; Luis Carlos Morales; Simonetta Sipione; Harley T Kurata
Journal:  Nat Commun       Date:  2018-10-24       Impact factor: 14.919

8.  Refining Genotypes and Phenotypes in KCNA2-Related Neurological Disorders.

Authors:  Jan H Döring; Julian Schröter; Jerome Jüngling; Saskia Biskup; Kerstin A Klotz; Thomas Bast; Tobias Dietel; G Christoph Korenke; Sophie Christoph; Heiko Brennenstuhl; Guido Rubboli; Rikke S Møller; Gaetan Lesca; Yves Chaix; Stefan Kölker; Georg F Hoffmann; Johannes R Lemke; Steffen Syrbe
Journal:  Int J Mol Sci       Date:  2021-03-10       Impact factor: 5.923

9.  BmK86-P1, a New Degradation Peptide with Desirable Thermostability and Kv1.2 Channel-Specific Activity from Traditional Chinese Scorpion Medicinal Material.

Authors:  Chenhu Qin; Xuhua Yang; Zheng Zuo; Liuting Yang; Fan Yang; Zhijian Cao; Zongyun Chen; Yingliang Wu
Journal:  Toxins (Basel)       Date:  2021-08-30       Impact factor: 4.546

  9 in total

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