Literature DB >> 27091480

Clinical laboratory standard capillary protein electrophoresis alerted of a low C3 state and lead to the identification of a Factor I deficiency due to a novel homozygous mutation.

Clara Franco-Jarava1, Roger Colobran2, Jaume Mestre-Torres3, Victor Vargas4, Ricardo Pujol-Borrell1, Manuel Hernández-González1.   

Abstract

Complement factor I (CFI) deficiency is typically associated to recurrent infections with encapsulated microorganisms and, less commonly, to autoimmunity. We report a 53-years old male who, in a routine control for non-alcoholic fatty liver disease, presented a flat beta-2 fraction at the capillary protein electropherogram. Patient's clinical records included multiple oropharyngeal infections since infancy and an episode of invasive meningococcal infection. Complement studies revealed reduced C3, low classical pathway activation and undetectable Factor I. CFI gene sequencing showed a novel inherited homozygous deletion of 5 nucleotides in exon 12, causing a frameshift leading to a truncated protein. This study points out that capillary protein electrophoresis can alert of possible states of low C3, which, once confirmed and common causes ruled out, can lead to CFI and other complement deficiency diagnosis. This is important since they constitute a still underestimated risk of invasive meningococcemia that can be greatly reduced by vaccination.
Copyright © 2016 European Federation of Immunological Societies. Published by Elsevier B.V. All rights reserved.

Entities:  

Keywords:  C3; Complement deficiency; Encapsulated bacterial infections; Factor I; Primary immunodeficiency; Sepsis; Serum protein electrophoresis

Mesh:

Substances:

Year:  2016        PMID: 27091480     DOI: 10.1016/j.imlet.2016.04.011

Source DB:  PubMed          Journal:  Immunol Lett        ISSN: 0165-2478            Impact factor:   3.685


  3 in total

1.  Early Versus Late Diagnosis of Complement Factor I Deficiency: Clinical Consequences Illustrated in Two Families with Novel Homozygous CFI Mutations.

Authors:  Clara Franco-Jarava; Elena Álvarez de la Campa; Xavier Solanich; Francisco Morandeira-Rego; Virgínia Mas-Bosch; Marina García-Prat; Xavier de la Cruz; Andrea Martín-Nalda; Pere Soler-Palacín; Manuel Hernández-González; Roger Colobran
Journal:  J Clin Immunol       Date:  2017-09-23       Impact factor: 8.317

2.  Classical and Non-classical Presentations of Complement Factor I Deficiency: Two Contrasting Cases Diagnosed via Genetic and Genomic Methods.

Authors:  Adrian M Shields; Alistair T Pagnamenta; Andrew J Pollard; Jenny C Taylor; Holger Allroggen; Smita Y Patel
Journal:  Front Immunol       Date:  2019-06-07       Impact factor: 7.561

3.  Newborn Screening for Presymptomatic Diagnosis of Complement and Phagocyte Deficiencies.

Authors:  Mahya Dezfouli; Sofia Bergström; Lillemor Skattum; Hassan Abolhassani; Maja Neiman; Monireh Torabi-Rahvar; Clara Franco Jarava; Andrea Martin-Nalda; Juana M Ferrer Balaguer; Charlotte A Slade; Anja Roos; Luis M Fernandez Pereira; Margarita López-Trascasa; Luis I Gonzalez-Granado; Luis M Allende-Martinez; Yumi Mizuno; Yusuke Yoshida; Vanda Friman; Åsa Lundgren; Asghar Aghamohammadi; Nima Rezaei; Manuel Hernández-Gonzalez; Ulrika von Döbeln; Lennart Truedsson; Toshiro Hara; Shigeaki Nonoyama; Jochen M Schwenk; Peter Nilsson; Lennart Hammarström
Journal:  Front Immunol       Date:  2020-03-17       Impact factor: 7.561

  3 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.